Peripheral CD19+ B-cell counts and infusion intervals as a surrogate for long-term B-cell depleting therapy in multiple sclerosis and neuromyelitis optica/neuromyelitis optica spectrum disorders

J Neurol. 2019 Jan;266(1):57-67. doi: 10.1007/s00415-018-9092-4. Epub 2018 Oct 30.

Abstract

Background: With ocrelizumab another drug is available for the treatment of multiple sclerosis (MS). Little is known on the long-term use of ocrelizumab on immune cell subsets, and no surrogate markers are available. Rituximab (RTX) has been in off-label use for the treatment of MS, neuromyelitis optica (NMO) and neuromyelitis optica spectrum disorder (NMOSD) for > 10 years.

Objective: We evaluated the long-term depletion and repopulation rate of peripheral CD19+ B-cells as a potential surrogate for the clinical outcome, and whether it may serve for dosage and time-to-infusion decision making.

Methods: We evaluated the CD19+ and CD4+/8+ T-cell counts in n = 153 patients treated with RTX (132 MS, 21 NMO/NMOSD). The dosages ranged from 250 to 2000 mg RTX. Depletion/repopulation rates of CD19+ B-cells as well as long-term total lymphocyte cell counts, were assessed and corroborated with EDSS, ARR (annualized relapse rate), MRI, and time to reinfusion.

Results: CD19+ B-cells' repopulation rate significantly varied depending on the dosage applied leading to individualized application intervals (mean 9.73 ± 0.528 months). Low/absent CD19+ B-cell counts were associated with reduced ARR, EDSS, and GD+-MRI-lesions. Long-term B-cell-depleting therapy led to a transiently skewed CD4+/8+ T-cell ratio due to reduced CD4+ T-cells and absolute lymphocyte counts, which recovered after the second cycle.

Conclusion: Our data suggest that CD19+ B-cell repopulation latency may serve as surrogate marker for individualized treatment strategies in MS and NMO/NMOSD, which proved clinically equally effective in our cohort as evaluated by previous studies.

Keywords: CD19+ B-cell counts; Monoclonal anti-CD20 antibody; Multiple sclerosis; Neuromyelitis optica; Neuromyelitis optica spectrum disorders.

MeSH terms

  • Adult
  • Antigens, CD19 / metabolism
  • B-Lymphocytes / immunology
  • Dose-Response Relationship, Immunologic
  • Female
  • Follow-Up Studies
  • Humans
  • Lymphocyte Count
  • Male
  • Middle Aged
  • Multiple Sclerosis / blood*
  • Multiple Sclerosis / diagnostic imaging
  • Multiple Sclerosis / immunology
  • Multiple Sclerosis / therapy*
  • Neuromyelitis Optica / blood*
  • Neuromyelitis Optica / diagnostic imaging
  • Neuromyelitis Optica / immunology
  • Neuromyelitis Optica / therapy*
  • T-Lymphocytes / immunology

Substances

  • Antigens, CD19
  • CD19 molecule, human