Long-term pulmonary outcomes and mortality in idiopathic inflammatory myopathies associated with interstitial lung disease

Clin Rheumatol. 2019 Mar;38(3):803-815. doi: 10.1007/s10067-018-4353-2. Epub 2018 Nov 3.

Abstract

Objective: To study prognostic factors in different types of idiopathic inflammatory myopathies (IIM) associated with interstitial lung disease (ILD).

Patients and methods: Multicenter retrospective study of a Spanish cohort of patients diagnosed with IIM. Patients were classified into four categories: polymyositis (PM), dermatomyositis (DM), antisynthetase syndrome (ASS), and overlap myositis (OM). Sociodemographic data, clinical characteristics, antibodies, and treatments were collected. Cox regression models were calculated to identify factors associated with mortality, the necessity for long-term oxygen therapy (LTOT), and deterioration in respiratory function tests (RFT).

Results: The number of patients included was 478, of whom 112 (23.4%) suffered from ILD: 17% PM, 16% DM, 45% ASS, and 22% OM. Factors associated with mortality in the multivariate analysis were clinically meaningful progression of ILD after 3 months (CMP 3m) (hazard ratio (HR) 9.48, p = 0.005), severe infections (HR 6.41, p = 0.016), heliotrope erythema (HR 31.1, p = 0.002), delay in diagnosis (HR 1.29; p = 0.011), and Raynaud's phenomenon (HR 11.9, p = 0.007). However, being female (HR 0.19, p = 0.044) and positivity solely for ANAs (HR 0.08, p = 0.008) presented a protective effect. CMP 3m (HR 22.7, p = 0.027) was associated with the need for LTOT, while basal aldolase (HR 0.90; p = 0.049) had a protective effect. Likewise, joint manifestations (HR 0.04, p = 0.034) were shown to reduce risk of deterioration in RFT.

Conclusions: CMP 3m, severe infections, delay in diagnosis, heliotrope erythema, and Raynaud's phenomenon were identified as factors of poor prognosis in different IIM associated with ILD.

Keywords: Interstitial lung disease; Myositis; Oxygen therapy; Prognosis; Respiratory function tests; Survival.

MeSH terms

  • Adolescent
  • Adult
  • Aged
  • Antibodies, Antinuclear / immunology
  • Delayed Diagnosis / statistics & numerical data
  • Dermatomyositis / epidemiology
  • Dermatomyositis / immunology
  • Dermatomyositis / physiopathology
  • Disease Progression
  • Erythema / epidemiology
  • Female
  • Fructose-Bisphosphate Aldolase / metabolism
  • Humans
  • Infections / epidemiology
  • Kaplan-Meier Estimate
  • Longitudinal Studies
  • Lung Diseases, Interstitial / epidemiology
  • Lung Diseases, Interstitial / physiopathology*
  • Lung Diseases, Interstitial / therapy
  • Male
  • Middle Aged
  • Mortality*
  • Multivariate Analysis
  • Myositis / epidemiology
  • Myositis / immunology
  • Myositis / physiopathology*
  • Oxygen Inhalation Therapy / statistics & numerical data*
  • Polymyositis / epidemiology
  • Polymyositis / immunology
  • Polymyositis / physiopathology
  • Prognosis
  • Proportional Hazards Models
  • Protective Factors
  • Pulmonary Diffusing Capacity
  • Raynaud Disease / epidemiology
  • Respiratory Function Tests
  • Retrospective Studies
  • Risk Factors
  • Sex Factors
  • Spain / epidemiology
  • Vital Capacity
  • Young Adult

Substances

  • Antibodies, Antinuclear
  • Fructose-Bisphosphate Aldolase

Supplementary concepts

  • Antisynthetase syndrome