Clinical, neuroimaging and therapeutic response in AQP4-positive NMO patients from India

Mult Scler Relat Disord. 2019 May:30:85-93. doi: 10.1016/j.msard.2019.01.032. Epub 2019 Feb 4.

Abstract

Background: Neuromyelitis Optica (NMO) is an autoimmune astrocytopathic disorder due to AQP4 antibodies.

Objectives: To analyse clinical, neuroimaging features in NMO patients and assess the efficacy of various therapeutics.

Methods: AQP4+ve NMO patients were diagnosed based on consensus diagnostic criteria.

Results: 101 AQP4+ve NMO patients were seen with female (90) predominance. Adult population (71.3%) formed the larger group followed by pediatric (19.8%) and late-onset (8.9%). Myelopathy (36.2%) was most commonly seen followed by optic neuritis (19.1%), brainstem (17.1%), opticomyelopathy (16.1%), area postrema involvement (10.5%) and encephalopathy (1%). Encephalopathy and brainstem/cerebellar involvement were most common in pediatric population while opticomyelopathy was more common in late-onset patients. Hyperintensities of lower medulla was seen in 67.3% subjects and 49.5% had involvement of obex. Differential T2 hyperintensity of the long segment myelitis was found in 30.7%. Plasmapheresis was given in 71 subjects followed by maintenance therapy. Most of them showed significant improvement with EDSS score of 1 in 30.7%.

Conclusions: Clinical manifestations in AQP4+ve NMO patients may vary depending on the age at onset of illness. MRI features affecting cervicomedullary junction, obex, differential T2 hyperintensities of the spinal cord may form a useful diagnostic clue. Plasmapheresis is helpful in achieving remission along with immunomodulation.

Keywords: Cervico-medullary junction; Mycophenolate mofetil; NMO; Neuromyelitis optica; Obex; Plasmapheresis; Rituximab.

MeSH terms

  • Adolescent
  • Adult
  • Aged
  • Aquaporin 4 / immunology*
  • Autoantibodies / immunology*
  • Child
  • Female
  • Humans
  • Immunosuppressive Agents / therapeutic use*
  • India
  • Magnetic Resonance Imaging
  • Male
  • Middle Aged
  • Neuromyelitis Optica* / immunology
  • Neuromyelitis Optica* / pathology
  • Neuromyelitis Optica* / physiopathology
  • Neuromyelitis Optica* / therapy
  • Plasmapheresis*
  • Severity of Illness Index
  • Young Adult

Substances

  • AQP4 protein, human
  • Aquaporin 4
  • Autoantibodies
  • Immunosuppressive Agents