Subarachnoid Hemorrhage with Concurrent Dural and Perimedullary Arteriovenous Fistulas at Craniocervical Junction: Case Report and Literature Review

World Neurosurg. 2019 Jul:127:331-334. doi: 10.1016/j.wneu.2019.02.079. Epub 2019 Feb 28.

Abstract

Background: The association between a dural arteriovenous fistula (dAVF) and perimedullary arteriovenous fistula (AVF) is rarely observed at the craniocervical junction (CCJ). We present a case of subarachnoid hemorrhage (SAH) with concurrent dAVF and perimedullary AVF at the CCJ. Here, we describe the cause of bleeding and the process of determining whether it was a varix or an arterial aneurysm.

Case description: A 69-year-old man with SAH visited the emergency department. A dAVF at the CCJ was detected on digital subtraction angiography (DSA). However, after 3 weeks, when the DSA was repeated, a perimedullary AVF and varix were identified. We performed an endovascular treatment, but because the perimedullary AVF remained, we performed a direct surgery. The patient was discharged without weakness, but this left abducens nerve palsy remained.

Conclusions: In recent reports, SAH caused by concurrent dAVF and perimedullary AVF raised the possibility of an arterial aneurysm. However, in this case, the possibility of venous bleeding was high and a varix rather than an aneurysm was observed. On the basis of the reported cases, concurrent dAVF and perimedullary AVF at the CCJ is a "middle-flow arteriovenous shunt" that may induce a varix or an arterial aneurysm.

Keywords: Craniocervical junction; Perimedullary AVF; dAVF.

Publication types

  • Case Reports
  • Review

MeSH terms

  • Aged
  • Central Nervous System Vascular Malformations / complications
  • Central Nervous System Vascular Malformations / diagnostic imaging
  • Central Nervous System Vascular Malformations / surgery*
  • Cervical Vertebrae / diagnostic imaging
  • Cervical Vertebrae / surgery*
  • Humans
  • Male
  • Medulla Oblongata / diagnostic imaging
  • Medulla Oblongata / surgery*
  • Skull Base / diagnostic imaging
  • Skull Base / surgery*
  • Subarachnoid Hemorrhage / complications
  • Subarachnoid Hemorrhage / diagnostic imaging
  • Subarachnoid Hemorrhage / surgery*