Drug Screening in Human PSC-Cardiac Organoids Identifies Pro-proliferative Compounds Acting via the Mevalonate Pathway

Cell Stem Cell. 2019 Jun 6;24(6):895-907.e6. doi: 10.1016/j.stem.2019.03.009. Epub 2019 Mar 28.

Abstract

We have previously developed a high-throughput bioengineered human cardiac organoid (hCO) platform, which provides functional contractile tissue with biological properties similar to native heart tissue, including mature, cell-cycle-arrested cardiomyocytes. In this study, we perform functional screening of 105 small molecules with pro-regenerative potential. Our findings reveal surprising discordance between our hCO system and traditional 2D assays. In addition, functional analyses uncovered detrimental effects of many hit compounds. Two pro-proliferative small molecules without detrimental impacts on cardiac function were identified. High-throughput proteomics in hCO revealed synergistic activation of the mevalonate pathway and a cell-cycle network by the pro-proliferative compounds. Cell-cycle reentry in hCO and in vivo required the mevalonate pathway as inhibition of the mevalonate pathway with a statin attenuated pro-proliferative effects. This study highlights the utility of human cardiac organoids for pro-regenerative drug development, including identification of underlying biological mechanisms and minimization of adverse side effects.

Keywords: cardiomyocyte proliferation; cholesterol; drug development; organoid; pluripotent stem cells; statin.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Cell Cycle
  • Cell Proliferation
  • Cells, Cultured
  • Drug Evaluation, Preclinical / methods*
  • High-Throughput Screening Assays
  • Humans
  • Hydroxymethylglutaryl-CoA Reductase Inhibitors / pharmacology
  • Mevalonic Acid / metabolism*
  • Myocardium / cytology*
  • Myocytes, Cardiac / drug effects
  • Myocytes, Cardiac / physiology*
  • Organ Culture Techniques
  • Organoids / cytology*
  • Proteomics
  • Regeneration
  • Signal Transduction

Substances

  • Hydroxymethylglutaryl-CoA Reductase Inhibitors
  • Mevalonic Acid