[A novel compound heterozygous mutation of GNPTAB gene underlying a case with mucolipidosis type II α/β]

Zhonghua Yi Xue Yi Chuan Xue Za Zhi. 2019 Jun 10;36(6):606-609. doi: 10.3760/cma.j.issn.1003-9406.2019.06.019.
[Article in Chinese]

Abstract

Objective: To analyze the clinical features and genetic mutations in a patient with mucolipidosis type II α/β by using next generation sequencing.

Methods: Clinical data of the patient was collected. Genomic DNA of the patient and her parents was extracted by a standard method. The patient was subjected to targeted sequencing using an Ion Ampliseq panel, which included genes related to mucolipidosis and mucopolysaccharidosis. Suspected mutations were verified by Sanger sequencing.

Results: Compound heterozygous mutations, namely c.1284+1G>T and c.1090C>T (p.Arg364*), were detected in the patient, which were respectively inherited from her mother and father. No other disease-causing mutation was detected in the patient. GNPTAB c.1090C>T was known to be pathogenic, while GNPTAB c.1284+1G>T is a novel mutation. The same mutations were not detected among 50 healthy controls.

Conclusion: The compound heterozygous mutations c.1284+1G>T and c.1090C>T (p.Arg364*) of GNPTAB gene probably account for the mucolipidosis type II α/β in the patient. NGS has a great value for the molecular diagnosis and typing of mucolipidosis.

Publication types

  • Case Reports

MeSH terms

  • Female
  • High-Throughput Nucleotide Sequencing
  • Humans
  • Mucolipidoses* / genetics
  • Mutation
  • Transferases (Other Substituted Phosphate Groups) / genetics*

Substances

  • Transferases (Other Substituted Phosphate Groups)
  • GNPTAB protein, human