The nucleoporin ELYS regulates nuclear size by controlling NPC number and nuclear import capacity

EMBO Rep. 2019 Jun;20(6):e47283. doi: 10.15252/embr.201847283. Epub 2019 May 13.

Abstract

How intracellular organelles acquire their characteristic sizes is a fundamental question in cell biology. Given stereotypical changes in nuclear size in cancer, it is important to understand the mechanisms that control nuclear size in human cells. Using a high-throughput imaging RNAi screen, we identify and mechanistically characterize ELYS, a nucleoporin required for post-mitotic nuclear pore complex (NPC) assembly, as a determinant of nuclear size in mammalian cells. ELYS knockdown results in small nuclei, reduced nuclear lamin B2 localization, lower NPC density, and decreased nuclear import. Increasing nuclear import by importin α overexpression rescues nuclear size and lamin B2 import, while inhibiting importin α/β-mediated nuclear import decreases nuclear size. Conversely, ELYS overexpression increases nuclear size, enriches nuclear lamin B2 at the nuclear periphery, and elevates NPC density and nuclear import. Consistent with these observations, knockdown or inhibition of exportin 1 increases nuclear size. Thus, we identify ELYS as a novel positive effector of mammalian nuclear size and propose that nuclear size is sensitive to NPC density and nuclear import capacity.

Keywords: ELYS; nuclear pore complex; nuclear size; nucleocytoplasmic transport; nucleus.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, N.I.H., Intramural

MeSH terms

  • Active Transport, Cell Nucleus
  • Biomarkers
  • Cell Line, Tumor
  • Cell Nucleus / genetics
  • Cell Nucleus / metabolism*
  • Cell Nucleus / pathology
  • DNA-Binding Proteins / genetics
  • DNA-Binding Proteins / metabolism*
  • Gene Expression Profiling
  • Gene Knockdown Techniques
  • Humans
  • Molecular Imaging
  • Nuclear Pore
  • Nuclear Pore Complex Proteins / genetics
  • Nuclear Pore Complex Proteins / metabolism*
  • Protein Binding
  • RNA Interference
  • RNA, Small Interfering / genetics
  • Transcription Factors / genetics
  • Transcription Factors / metabolism*

Substances

  • AHCTF1 protein, human
  • Biomarkers
  • DNA-Binding Proteins
  • Nuclear Pore Complex Proteins
  • RNA, Small Interfering
  • Transcription Factors