Renal ciliopathies

Curr Opin Genet Dev. 2019 Jun:56:49-60. doi: 10.1016/j.gde.2019.07.005. Epub 2019 Aug 13.

Abstract

Renal ciliopathies are a group of disorders characterised by nephronophthisis, cystic kidneys or renal cystic dysplasia whose underlying disease pathogenesis is related to abnormal structure or function of the primary cilia complex. The number of renal ciliopathies continues to expand as genomic and genetic approaches identify novel causes. This in turn provides new opportunities to explore disease mechanisms and therapeutic approaches to target cystic kidney disease and other associated phenotypes. Here we review recent advances in the field of renal ciliopathies and how these allow new insights into this fascinating spectrum of diseases.

Publication types

  • Research Support, Non-U.S. Gov't
  • Review

MeSH terms

  • Cilia / genetics*
  • Ciliopathies / genetics*
  • Ciliopathies / pathology
  • Ciliopathies / therapy
  • Genetic Predisposition to Disease / genetics*
  • Humans
  • Kidney / metabolism*
  • Kidney / pathology
  • Kidney Diseases, Cystic / genetics*
  • Kidney Diseases, Cystic / pathology
  • Kidney Diseases, Cystic / therapy
  • Mutation
  • Phenotype
  • Sequence Analysis, DNA / methods
  • Signal Transduction / genetics