[Molecular cytogenetic diagnosis of a case with ring chromosome 18 syndrome]

Zhonghua Yi Xue Yi Chuan Xue Za Zhi. 2019 Oct 10;36(10):1010-1014. doi: 10.3760/cma.j.issn.1003-9406.2019.10.015.
[Article in Chinese]

Abstract

Objective: To explore the genetic basis for a child with developmental delay and congenital syndactyly.

Methods: G-banding chromosomal karyotyping and chromosomal microarray analysis (CMA) were performed on peripheral blood sample from the child.

Results: The child was ascertained as 46, XY, r(18)[52]/45,XY,?18[3]. A 18q21.32-q23 deletion was identified by CMA with a size of 19.85 Mb, which has encompassed 99 genes including CTDP1, TXNL4A, TSHZ1, PIGN, RTTN, TNFRSF11A, KDSR and CYB5A.

Conclusion: Clinical phenotype of the patient with ring chromosome 18 is associated with the size of the euchromatin loss and involved genes. As a useful complement to conventional karyotyping, CMA has provided an powerful tool for delineating complex chromosomal aberrations.

MeSH terms

  • Child
  • Chromosome Aberrations*
  • Chromosomes, Human, Pair 18 / genetics
  • Cytogenetics
  • Developmental Disabilities / genetics*
  • Humans
  • Karyotyping
  • Ring Chromosomes
  • Syndactyly / genetics*

Supplementary concepts

  • Chromosome 18 ring