Ewing sarcoma in a child with neurofibromatosis type 1

Cold Spring Harb Mol Case Stud. 2019 Oct 23;5(5):a004580. doi: 10.1101/mcs.a004580. Print 2019 Oct.

Abstract

We report here on a case of Ewing sarcoma (ES) occurring in a child with neurofibromatosis type 1. The sarcoma had an EWSR1-ERG translocation as well as loss of the remaining wild-type allele of NF1. Loss of the NF1 wild-type allele in the tumor suggests that activation of the Ras pathway contributed to its evolution. Review of available public data suggests that secondary mutations in the Ras pathway are found in ∼3% of ESs. This case suggests that Ras pathway activation may play a role in tumor progression in a subset of ESs.

Keywords: Ewing's sarcoma; multiple cafe-au-lait spots; neurofibromas.

Publication types

  • Case Reports

MeSH terms

  • Child, Preschool
  • Family
  • Female
  • Humans
  • Mutation
  • Neurofibromatosis 1 / complications*
  • Neurofibromatosis 1 / genetics
  • Sarcoma, Ewing / diagnosis*
  • Sarcoma, Ewing / genetics*
  • ras Proteins / metabolism

Substances

  • ras Proteins