Positive oligoclonal bands and CSF pleocytosis in narcolepsy type 1: A case report supporting the immune-mediated hypothesis

J Neuroimmunol. 2020 Feb 15:339:577111. doi: 10.1016/j.jneuroim.2019.577111. Epub 2019 Nov 14.

Abstract

Narcolepsy-type 1 is a neurological sleep-disorder caused by a selective loss of hypothalamic orexin/hypocretin-producing neurons whose underlying mechanism is considered to be immune-mediated. We report the case of a 16 year-old girl with excessive daytime sleepiness, hypnagogic/hypnopompic hallucinations and cataplexy, fulfilling narcolepsy-type 1 diagnostic criteria. She was HLA-DQB1*06:02/DQA1*01:02 positive. CSF analysis demonstrated positive IgG oligoclonal bands, pleocytosis and hypocretin-1 below detection limit. Other autoimmune processes were excluded, including autoimmune encephalitis. After treatment with intravenous immunoglobulins sleep-related hallucinations transiently improved for a month. This case's CSF inflammatory findings support the role of neuroinflammation in narcolepsy-type 1 development in genetically predisposed patients.

Keywords: Autoimmune diseases; Narcolepsy.

Publication types

  • Case Reports

MeSH terms

  • Adolescent
  • Biomarkers / cerebrospinal fluid
  • Female
  • Humans
  • Immunoglobulins, Intravenous / therapeutic use
  • Leukocytosis / cerebrospinal fluid*
  • Leukocytosis / diagnosis*
  • Leukocytosis / drug therapy
  • Narcolepsy / cerebrospinal fluid*
  • Narcolepsy / diagnosis*
  • Narcolepsy / drug therapy
  • Oligoclonal Bands / cerebrospinal fluid*

Substances

  • Biomarkers
  • Immunoglobulins, Intravenous
  • Oligoclonal Bands

Supplementary concepts

  • Narcolepsy 1