Granulomatosis-associated myositis: High prevalence of sporadic inclusion body myositis

Neurology. 2020 Mar 3;94(9):e910-e920. doi: 10.1212/WNL.0000000000008863. Epub 2019 Dec 27.

Abstract

Objective: To refine the predictive significance of muscle granuloma in patients with myositis.

Methods: A group of 23 patients with myositis and granuloma on muscle biopsy (granuloma-myositis) from 8 French and Belgian centers was analyzed and compared with (1) a group of 23 patients with myositis without identified granuloma (control-myositis) randomly sampled in each center and (2) a group of 20 patients with sporadic inclusion body myositis (sIBM) without identified granuloma (control-sIBM).

Results: All but 2 patients with granuloma-myositis had extramuscular involvement, including signs common in sarcoidosis that were systematically absent in the control-myositis and the control-sIBM groups. Almost half of patients with granuloma-myositis matched the diagnostic criteria for sIBM. In these patients, other than the granuloma, the characteristics of the myopathy and its nonresponse to treatment were similar to the control-sIBM patients. Aside from 1 patient with myositis overlapping with systemic sclerosis, the remaining patients with granuloma-myositis did not match the criteria for a well-defined myositis subtype, suggesting pure sarcoidosis. Matching criteria for sIBM was the sole feature independently associated with nonresponse to myopathy treatment in patients with granuloma-myositis.

Conclusion: Patients with granuloma-myositis should be carefully screened for sIBM associated with sarcoidosis in order to best tailor their care.

MeSH terms

  • Adult
  • Aged
  • Aged, 80 and over
  • Belgium / epidemiology
  • Comorbidity
  • Female
  • France / epidemiology
  • Granuloma / epidemiology*
  • Humans
  • Male
  • Middle Aged
  • Muscle, Skeletal / pathology*
  • Myositis / epidemiology*
  • Myositis, Inclusion Body / pathology*
  • Prevalence
  • Sarcoidosis / epidemiology*