Once in a Blue Moon, a Very Rare Coexistence of Glutaric Acidemia Type I and Mucopolysaccharidosis Type IIIB in a Patient

Iran Biomed J. 2020 May;24(3):201-5. doi: 10.29252/ibj.24.3.201. Epub 2019 Nov 27.

Abstract

Background: Glutaric acidemia (GAI) and mucopolysaccharidosis type IIIB (MPSIIIB) are two rare genetic disorders caused by pathogenic variants in two different genes. Here, we report a coexistence of these two different rare disorders in an individual.

Methods: A four-year-old Iranian boy born to first-cousin parents suspected to have MPSIIIB and/or GAI was investigated in this study. Targeted genomic enrichment and next-generation sequencing were used to examine genes related to MPS and GA. Sanger sequencing was performed to confirm the results.

Results: Two homozygous likely pathogenic variants in α-N-acetylglucosaminidase (NAGLU) and GCDH genes were found and confirmed in the proband.

Conclusion: A combination of specific features of two different diseases in a patient has been reported here. More studies on this case and similar cases can provide more information about the effect of simultaneous pathogenic variants in different genes.

Keywords: Genes; Iran; Mucopolysaccharidoses.

Publication types

  • Case Reports

MeSH terms

  • Amino Acid Metabolism, Inborn Errors / complications*
  • Base Sequence
  • Brain Diseases, Metabolic / complications*
  • Child, Preschool
  • Female
  • Glutaryl-CoA Dehydrogenase / deficiency*
  • Humans
  • Male
  • Mucopolysaccharidosis III / complications*
  • Pedigree

Substances

  • Glutaryl-CoA Dehydrogenase

Supplementary concepts

  • Glutaric Acidemia I