Introduction: Severe penile torsion of 180° associated with hypospadias is a rare entity. Knowledge of penile anatomy and pathology are necessary as the diagnosis could be missed.
Case presentation: We report a case of severe 180° penile torsion with distal hypospadias that was mistaken for an epispadias which was corrected with surgery.
Conclusion: Tubularized incised plate urethroplasty and dartos flap rotation provided satisfactory result for this association.
Keywords: dartos flap; hypospadias; penile torsion.
© 2019 The Authors. IJU Case Reports published by John Wiley & Sons Australia, Ltd on behalf of the Japanese Urological Association.