LPL deletion is associated with poorer response to ibrutinib-based treatments and overall survival in TP53-deleted chronic lymphocytic leukemia

Ann Hematol. 2020 Oct;99(10):2343-2349. doi: 10.1007/s00277-020-04223-y. Epub 2020 Aug 24.

Abstract

Ibrutinib-based therapy represents a recent success in managing high-risk CLL patients with 17p/TP53 deletion. However, a subset of CLL patients are resistant to therapy. Deletion of lipoprotein lipase (LPL) has been postulated as a potential evasion mechanism to ibrutinib-based therapy. In this study, we assessed for LPL deletion by fluorescence in situ hybridization in 176 consecutive CLL patients with 17p/TP53 deletion. LPL deletion was detected in 35 (20%) of CLL patients. Patients with LPL deletion (del) showed a higher frequency of CD38 expression but have comparable frequencies of somatic hypermutation and ZAP-70 expression compared with patients with normal (nml) LPL. Gene mutation analysis showed that TP53 was mutated in 68% of LPL-del versus 91% of LPL-nml patients. The overall response to ibrutinib-based therapy was 57%, including 37% complete remission (CR) and 20% partial remission (PR) in patients with LPL-del versus 90% (56% CR and 34% PR) in patients with LPL-nml (p < 0.001). LPL-del patients also showed a poorer overall survival (OS) compared with patients with LPL-nml (median OS, 236 months versus undefined, p < 0.001). In summary, the data presented establish an association between LPL deletion, resistance to ibrutinib-based therapy, and poorer overall survival in TP53-deleted CLL patients. We suggest that LPL deletion might be utilized as a biomarker for risk stratification and to predict therapeutic response in this high-risk group of CLL patients.

Keywords: Chronic lymphocytic leukemia (CLL); Ibrutinib; Lipoprotein lipase (LPL); TP53.

MeSH terms

  • Adenine / analogs & derivatives
  • Adult
  • Aged
  • Aged, 80 and over
  • Antineoplastic Agents / therapeutic use*
  • Antineoplastic Combined Chemotherapy Protocols / therapeutic use
  • Biomarkers, Tumor
  • Bridged Bicyclo Compounds, Heterocyclic / administration & dosage
  • Drug Resistance, Neoplasm / genetics*
  • Female
  • Gene Deletion*
  • Genes, p53
  • Humans
  • In Situ Hybridization, Fluorescence
  • Kaplan-Meier Estimate
  • Leukemia, Lymphocytic, Chronic, B-Cell / drug therapy
  • Leukemia, Lymphocytic, Chronic, B-Cell / genetics*
  • Leukemia, Lymphocytic, Chronic, B-Cell / mortality
  • Lipoprotein Lipase / deficiency*
  • Lipoprotein Lipase / genetics
  • Lipoprotein Lipase / physiology
  • Male
  • Middle Aged
  • Neoplasm Proteins / biosynthesis
  • Neoplasm Proteins / genetics
  • Piperidines
  • Proportional Hazards Models
  • Protein Kinase Inhibitors / therapeutic use*
  • Pyrazoles / administration & dosage
  • Pyrazoles / therapeutic use*
  • Pyrimidines / administration & dosage
  • Pyrimidines / therapeutic use*
  • Risk Assessment
  • Rituximab / administration & dosage
  • Sulfonamides / administration & dosage
  • Treatment Outcome
  • Tumor Suppressor Protein p53 / deficiency
  • ZAP-70 Protein-Tyrosine Kinase / biosynthesis
  • ZAP-70 Protein-Tyrosine Kinase / genetics

Substances

  • Antineoplastic Agents
  • Biomarkers, Tumor
  • Bridged Bicyclo Compounds, Heterocyclic
  • Neoplasm Proteins
  • Piperidines
  • Protein Kinase Inhibitors
  • Pyrazoles
  • Pyrimidines
  • Sulfonamides
  • TP53 protein, human
  • Tumor Suppressor Protein p53
  • ibrutinib
  • Rituximab
  • ZAP-70 Protein-Tyrosine Kinase
  • ZAP70 protein, human
  • LPL protein, human
  • Lipoprotein Lipase
  • Adenine
  • venetoclax