Human papilloma virus (HPV) integration signature in Cervical Cancer: identification of MACROD2 gene as HPV hot spot integration site

Br J Cancer. 2021 Feb;124(4):777-785. doi: 10.1038/s41416-020-01153-4. Epub 2020 Nov 16.

Abstract

Background: Cervical cancer (CC) remains a leading cause of gynaecological cancer-related mortality with infection by human papilloma virus (HPV) being the most important risk factor. We analysed the association between different viral integration signatures, clinical parameters and outcome in pre-treated CCs.

Methods: Different integration signatures were identified using HPV double capture followed by next-generation sequencing (NGS) in 272 CC patients from the BioRAIDs study [NCT02428842]. Correlations between HPV integration signatures and clinical, biological and molecular features were assessed.

Results: Episomal HPV was much less frequent in CC as compared to anal carcinoma (p < 0.0001). We identified >300 different HPV-chromosomal junctions (inter- or intra-genic). The most frequent integration site in CC was in MACROD2 gene followed by MIPOL1/TTC6 and TP63. HPV integration signatures were not associated with histological subtype, FIGO staging, treatment or PFS. HPVs were more frequently episomal in PIK3CA mutated tumours (p = 0.023). Viral integration type was dependent on HPV genotype (p < 0.0001); HPV18 and HPV45 being always integrated. High HPV copy number was associated with longer PFS (p = 0.011).

Conclusions: This is to our knowledge the first study assessing the prognostic value of HPV integration in a prospectively annotated CC cohort, which detects a hotspot of HPV integration at MACROD2; involved in impaired PARP1 activity and chromosome instability.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Carcinoma, Squamous Cell / genetics
  • Carcinoma, Squamous Cell / virology
  • Class I Phosphatidylinositol 3-Kinases / genetics
  • DNA Repair Enzymes / genetics*
  • Female
  • Humans
  • Hydrolases / genetics*
  • Kallikreins / genetics
  • Middle Aged
  • Papillomaviridae / genetics
  • Papillomaviridae / physiology*
  • Papillomavirus Infections / genetics
  • Papillomavirus Infections / virology*
  • Progression-Free Survival
  • Prostate-Specific Antigen / genetics
  • Uterine Cervical Neoplasms / genetics
  • Uterine Cervical Neoplasms / virology*
  • Virus Integration / genetics*

Substances

  • MACROD2 protein, human
  • Class I Phosphatidylinositol 3-Kinases
  • PIK3CA protein, human
  • Hydrolases
  • KLK3 protein, human
  • Kallikreins
  • Prostate-Specific Antigen
  • DNA Repair Enzymes