Compound Heterozygosity for a Novel Mutation Codon 104 (-A) (HBB: c.313delA) and Codons 41/42 (-CTTT) (HBB: c.126_129delCTTT) Leading to β-Thalassemia Major in a Chinese Family

Hemoglobin. 2020 Nov;44(6):402-405. doi: 10.1080/03630269.2020.1843482. Epub 2020 Nov 16.

Abstract

β-Thalassemia (β-thal) is a hereditary blood disorder characterized by the reduced or absent synthesis of β-globin chains. Here, we report a case of severe thalassemia with compound heterozygosity for a novel deletion mutation at codon 104 (-A) (HBB: c.313delA) and codons 41/42 (-CTTT) (HBB: c.126_129delCTTT) on the β-globin gene (HBB), and a coinheritance of the -α4.2 (leftward) deletion on the α-globin gene cluster. The proband was a 12-year-old boy, and four other family members were involved in this study. This novel frameshift mutation caused classical β-thal trait in the heterozygote and a transfusion-dependent form of β-thal major (β-TM) in compound heterozygosity with other β0 mutations.

Keywords: HBB gene; compound heterozygote; frameshift mutation; nucleotide sequencing; β-Thalassemia.

Publication types

  • Case Reports

MeSH terms

  • Alleles
  • Amino Acid Substitution
  • Asian People / genetics*
  • Child
  • China
  • Codon*
  • DNA Mutational Analysis
  • Erythrocyte Indices
  • Exons
  • Female
  • Frameshift Mutation
  • Heterozygote*
  • Humans
  • Male
  • Mutation*
  • Pedigree
  • beta-Globins / genetics*
  • beta-Thalassemia / diagnosis*
  • beta-Thalassemia / genetics*

Substances

  • Codon
  • beta-Globins