Primary Immunodeficiencies in India: Molecular Diagnosis and the Role of Next-Generation Sequencing

J Clin Immunol. 2021 Feb;41(2):393-413. doi: 10.1007/s10875-020-00923-2. Epub 2020 Nov 23.

Abstract

Primary immunodeficiency diseases (PIDs) are a group of clinically and genetically heterogeneous disorders showing ethnic and geographic diversities. Next-generation sequencing (NGS) is a comprehensive tool to diagnose PID. Although PID is common in India, data on the genetic spectrum of PIDs are limited due to financial restrictions. The study aims to characterize the clinical and genetic spectrum of PID patients in India and highlight the importance of a cost-effective targeted gene panel sequencing approach for PID in a resource-limited setting. The study includes 229 patients with clinical and laboratory features suggestive of PIDs. Mutation analysis was done by Sanger sequencing and NGS targeting a customized panel of genes. Pathogenic variants were identified in 97 patients involving 42 different genes with BTK and IL12RB1 being the most common mutated genes. Autosomal recessive and X-linked recessive inheritance were seen in 51.6% and 23.7% of patients. Mendelian susceptibility to mycobacterial diseases (MSMD) and IL12RB1 mutations was more common in our population compared to the Western world and the Middle East. Two patients with hypomorphic RAG1 mutations and one female with skewed CYBB mutation were also identified. Another 40 patients had variants classified as variants of uncertain significance (VUS). The study shows that targeted NGS is an effective diagnostic strategy for PIDs in countries with limited diagnostic resources. Molecular diagnosis of PID helps in genetic counseling and to make therapeutic decisions including the need for a stem cell transplantation.

Keywords: India; Primary immunodeficiency; clinical exome sequencing; mutations; next-generation sequencing; targeted gene panel.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adolescent
  • Adult
  • Child
  • Child, Preschool
  • DNA Mutational Analysis / methods
  • Female
  • Genetic Testing / methods
  • High-Throughput Nucleotide Sequencing / methods*
  • Humans
  • India
  • Infant
  • Infant, Newborn
  • Male
  • Mutation / genetics
  • Pathology, Molecular / methods*
  • Primary Immunodeficiency Diseases / diagnosis*
  • Primary Immunodeficiency Diseases / genetics*
  • Young Adult