The phenotype caused by recessive variations in SLC25A22: Report of a new case and literature review

Arch Pediatr. 2021 Jan;28(1):87-92. doi: 10.1016/j.arcped.2020.10.015. Epub 2020 Dec 17.

Abstract

We describe the clinical, electroencephalography (EEG), and developmental features of a patient with developmental and epileptic encephalopathy due to a homozygous pathogenic variation of mitochondrial glutamate/H+ symporter SLC25A22. Epilepsy began during the first week of life with focal onset seizures. Interictal EEG revealed a suppression-burst pattern with extensive periods of non-activity. The prospective follow-up confirmed developmental encephalopathy as well as ongoing active epilepsy and almost no sign of development at 8 years of age. We confirm in the following paper that SLC25A22 recessive variations may cause a severe developmental and epileptic encephalopathy characterized by a suppression-burst pattern. On the basis of an in-depth literature review, we also provide an overview of this rare genetic cause of neonatal onset epilepsy.

Keywords: Early developmental and epileptic encephalopathy; Myoclonic seizures; SLC25A22; Suppression-burst.

Publication types

  • Case Reports
  • Review

MeSH terms

  • Brain Diseases / diagnosis*
  • Brain Diseases / genetics
  • Child
  • Child, Preschool
  • Developmental Disabilities / diagnosis*
  • Developmental Disabilities / genetics
  • Electroencephalography
  • Epilepsy / diagnosis*
  • Epilepsy / genetics
  • Female
  • Genes, Recessive
  • Homozygote
  • Humans
  • Infant
  • Infant, Newborn
  • Mitochondrial Membrane Transport Proteins / genetics*
  • Mutation
  • Phenotype*

Substances

  • Mitochondrial Membrane Transport Proteins
  • SLC25A22 protein, human