Characterization of autoantibodies, immunophenotype and autoimmune disease in a prospective cohort of patients with idiopathic CD4 lymphocytopenia

Clin Immunol. 2021 Mar:224:108664. doi: 10.1016/j.clim.2021.108664. Epub 2021 Jan 7.

Abstract

Objective: Characterize autoantibodies and autoimmune diseases in a prospective cohort of patients with Idiopathic CD4 Lymphocytopenia (ICL) a rare immunodeficiency characterized by an absolute CD4+ T count of <300 cells/μl in the absence of HIV or HTLV infection.

Methods: Single-Center prospective study of 67 patients conducted over an 11-year period. Rheumatologic evaluation and measurement of autoantibodies were systematically conducted, and flow cytometry of immune cell subsets was performed in a subset of patients.

Results: 54% of referred patients had clinical evidence of autoimmunity, with 34% having at least one autoimmune disease, most commonly autoimmune thyroid disease. 19%, had autoantibodies or incomplete features of autoimmune disease. Patients with autoimmune disease had more elevated serum immunoglobulins, and more effector memory T cells than those without autoimmunity.

Conclusions: Evidence of autoimmunity, including autoimmune diseases, is more prevalent in ICL than the general population, and should be considered part of this syndrome.

Keywords: Autoantibody; Autoimmunity; Idiopathic CD4 lymphocytopenia; Opportunistic infections.

Publication types

  • Research Support, N.I.H., Intramural

MeSH terms

  • Adult
  • Aged
  • Autoantibodies / analysis*
  • Autoimmune Diseases / complications
  • Autoimmune Diseases / immunology*
  • Cohort Studies
  • Communicable Diseases / complications
  • Female
  • Humans
  • Immunophenotyping / methods*
  • Male
  • Middle Aged
  • Prospective Studies
  • T-Lymphocytopenia, Idiopathic CD4-Positive / complications
  • T-Lymphocytopenia, Idiopathic CD4-Positive / immunology*
  • Young Adult

Substances

  • Autoantibodies