Hippocampal Involvement With Vigabatrin-Related MRI Signal Abnormalities in Patients With Infantile Spasms: A Novel Finding

J Child Neurol. 2021 Jun;36(7):575-582. doi: 10.1177/0883073820985395. Epub 2021 Jan 12.

Abstract

Background: In a subset of infants exhibiting typical vigabatrin-related magnetic resonance imaging (MRI) changes, the authors observed additional hippocampal signal abnormalities. The authors investigated occurrence and significance of additional signal abnormalities.

Methods: A retrospective review of infantile spasms patients with typical vigabatrin-related MRI abnormalities was performed. Atypical features included signal changes unilaterally or at previously unreported sites. Comparisons were made between patients with and without atypical features.

Results: In all, 26/55 (47%) exhibited typical vigabatrin-related MRI changes, with additional signal abnormalities in the hippocampi in 6 of 26. On follow-up, evolution of hippocampal signal changes paralleled changes at typical locations in 4 patients. Two patients, clinically well, without follow-up MRI. Patients with and without additional hippocampal signal changes did not differ with respect to clinical factors, including seizure status. One patient had unilateral thalamic/cerebral peduncle signal abnormality along with typical vigabatrin changes.

Conclusions: Hippocampal changes seen in subset of patients with typical vigabatrin-related changes may be attributable to vigabatrin exposure in the appropriate circumstance.

Keywords: hippocampus; infantile spasms; vigabatrin-related MRI changes.

MeSH terms

  • Anticonvulsants / therapeutic use*
  • Female
  • Hippocampus / diagnostic imaging*
  • Hippocampus / drug effects*
  • Hippocampus / pathology
  • Humans
  • Infant
  • Magnetic Resonance Imaging
  • Male
  • Retrospective Studies
  • Spasms, Infantile / diagnostic imaging*
  • Spasms, Infantile / drug therapy*
  • Vigabatrin / therapeutic use*

Substances

  • Anticonvulsants
  • Vigabatrin