Classic Kaposi sarcoma in a patient of Miao ethnicity followed up for 7 years: a case report

J Med Case Rep. 2021 Apr 19;15(1):179. doi: 10.1186/s13256-021-02777-7.

Abstract

Background: Classic Kaposi sarcoma (CKS) is a vascular sarcoma associated with human herpesvirus 8 (HHV-8), which is known to be more common in Mediterranean elderly men and is characterized by indolent clinical behavior. Xinjiang province in China is considered an endemic region for Kaposi's sarcoma-associated herpesvirus (KSHV), with higher incidence among adults of Kazak and Uyghur ethnicities. Cases of CKS are rarely reported in inland China. Here, we followed a case of CKS for 7 years in a patient of Miao ethnic background in southwestern China.

Case presentation: A 63-year-old Miao (southwestern China) man was initially diagnosed with CKS in 2010, having a history of limb lesions for 37 years, with left eyelid and binaural lesions for 9 years. He did not have sexual contact with men and was human immunodeficiency virus (HIV)-negative. Due to his lumbago and fever, spinal tuberculosis in the lumbar vertebra was highly suspected after computed tomography (CT) scan. However, diagnostic antituberculosis treatment for 4 weeks failed. The patient was followed up in 2016, when the rash was recovering as the systemic symptoms improved. A new CT was performed, which showed a partial response despite the absence of any medical treatment. The open reading frame (ORF)-K1 of KSHV from skin tissue of the foot was amplified and sequenced, and K1 belonged to subtype A. This genotype is consistent with the typical subtype present in Xinjiang.

Conclusions: We describe spontaneous partial regression of CKS in a patient of Miao ethnicity in inland China. Our sample may represent an unknown, novel genotype. Surveillance and regulating the immune state may represent a valuable approach for this rare disease.

Keywords: Ethnic groups; Genotype; Human herpesvirus 8; Kaposi sarcoma; Tomography.

Publication types

  • Case Reports

MeSH terms

  • Adult
  • Aged
  • China
  • Ethnicity
  • Genome, Viral
  • Genotype
  • Herpesvirus 8, Human / classification
  • Herpesvirus 8, Human / genetics*
  • Herpesvirus 8, Human / isolation & purification*
  • Humans
  • Male
  • Membrane Proteins
  • Middle Aged
  • Sarcoma, Kaposi / pathology*
  • Sarcoma, Kaposi / virology
  • Skin Neoplasms / pathology*
  • Skin Neoplasms / virology
  • Viral Envelope Proteins / classification
  • Viral Envelope Proteins / genetics

Substances

  • Membrane Proteins
  • ORF-K1 protein, Human herpesvirus 8
  • Viral Envelope Proteins