Hormonal tumor mapping for liver metastases of gastroenteropancreatic neuroendocrine neoplasms: a novel therapeutic strategy

J Cancer Res Clin Oncol. 2022 Mar;148(3):697-706. doi: 10.1007/s00432-021-03650-2. Epub 2021 Apr 27.

Abstract

Purpose: In patients with metastatic functional gastroenteropancreatic neuroendocrine neoplasms (GEP-NENs), it is unknown what degree of tumor reduction is required to eliminate hormonal symptoms. We aimed to reduce hormonal symptoms derived from advanced GEP-NENs by efficient minimal intervention, constructing a hormonal tumor map of liver metastases.

Methods: Between 2013 and 2019, we treated 12 insulinoma or gastrinoma patients with liver metastases. Liver segments containing hormone-producing tumors were identified by injecting calcium gluconate via the hepatic arteries and monitoring the change in serum hormone concentration in the three hepatic veins. A greater-than-twofold increase in hormone concentration indicated a tumor-feeding vessel.

Results: Cases included eight insulinomas and four gastrinomas. Primary lesions were functional in three patients and nonfunctional in 9. Nine patients showed hormonal step-up indicating the presence of functional lesions; eight showed step-up in tumor-bearing liver segments, while one with synchronous liver metastases showed step-up only in the pancreatic region. Five patients underwent surgery. Serum hormone concentration decreased markedly after removing the culprit lesions in 3; immediate improvement in hormonal symptoms was achieved in all patients. Three patients with previous surgical treatment who showed step-up underwent transcatheter arterial embolization, achieving temporary improvement of hormonal symptoms. Four patients showed unclear localization of the hormone-producing tumors; treatment options were limited, resulting in poor outcomes.

Conclusion: Hormonal tumor mapping demonstrated heterogeneity in hormone production among primary and metastatic tumors of GEP-NENs. Minimally invasive treatment based on hormonal mapping may be a viable alternative to conventional cytoreduction.

Keywords: Functional GEP-NENs; Hormonal heterogeneity; Liver metastases; Neuroendocrine neoplasms.

Publication types

  • Case Reports

MeSH terms

  • Adult
  • Aged
  • Female
  • Follow-Up Studies
  • Gastrinoma / blood
  • Gastrinoma / pathology*
  • Gastrinoma / surgery
  • Hormones / blood*
  • Humans
  • Insulinoma / blood
  • Insulinoma / pathology*
  • Insulinoma / surgery
  • Intestinal Neoplasms / blood
  • Intestinal Neoplasms / pathology*
  • Intestinal Neoplasms / surgery
  • Liver Neoplasms / blood
  • Liver Neoplasms / secondary*
  • Liver Neoplasms / surgery
  • Male
  • Middle Aged
  • Neuroendocrine Tumors / blood
  • Neuroendocrine Tumors / pathology*
  • Neuroendocrine Tumors / surgery
  • Pancreatic Neoplasms / blood
  • Pancreatic Neoplasms / pathology*
  • Pancreatic Neoplasms / surgery
  • Prognosis
  • Retrospective Studies
  • Stomach Neoplasms / blood
  • Stomach Neoplasms / pathology*
  • Stomach Neoplasms / surgery

Substances

  • Hormones

Supplementary concepts

  • Gastro-enteropancreatic neuroendocrine tumor