Novel Patched 1 Mutations in Patients with Gorlin-Goltz Syndrome Strategic Treated by Smoothened Inhibitor

Ann Dermatol. 2018 Oct;30(5):597-601. doi: 10.5021/ad.2018.30.5.597. Epub 2018 Aug 28.

Abstract

We studied a family with Gorlin-Goltz syndrome. The novel mutations of our cases were located on the 21st exon of the PTCH1 gene (c.3450C>G). The father, who received a strategic 56-day vismodegib treatment for disease control, was the first patient with Gorlin syndrome treated with the hedgehog inhibitor in Taiwan. The lesions regressed gradually, with scar formation, and were subsequently removed via a wide excision. Further details are provided below.

Keywords: Basal cell nevus syndrome; PTCH protein; Vismodegib.

Publication types

  • Case Reports