A functional genomics pipeline identifies pleiotropy and cross-tissue effects within obesity-associated GWAS loci

Nat Commun. 2021 Sep 6;12(1):5253. doi: 10.1038/s41467-021-25614-3.

Abstract

Genome-wide association studies (GWAS) have identified many disease-associated variants, yet mechanisms underlying these associations remain unclear. To understand obesity-associated variants, we generate gene regulatory annotations in adipocytes and hypothalamic neurons across cellular differentiation stages. We then test variants in 97 obesity-associated loci using a massively parallel reporter assay and identify putatively causal variants that display cell type specific or cross-tissue enhancer-modulating properties. Integrating these variants with gene regulatory information suggests genes that underlie obesity GWAS associations. We also investigate a complex genomic interval on 16p11.2 where two independent loci exhibit megabase-range, cross-locus chromatin interactions. We demonstrate that variants within these two loci regulate a shared gene set. Together, our data support a model where GWAS loci contain variants that alter enhancer activity across tissues, potentially with temporally restricted effects, to impact the expression of multiple genes. This complex model has broad implications for ongoing efforts to understand GWAS.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adipocytes / cytology
  • Adipocytes / physiology*
  • Arrhythmias, Cardiac / genetics
  • Arrhythmias, Cardiac / pathology
  • Enhancer Elements, Genetic*
  • Genetic Diseases, X-Linked / genetics
  • Genetic Diseases, X-Linked / pathology
  • Genetic Pleiotropy*
  • Genome-Wide Association Study
  • Gigantism / genetics
  • Gigantism / pathology
  • Heart Defects, Congenital / genetics
  • Heart Defects, Congenital / pathology
  • Humans
  • Hypothalamus / physiology
  • Intellectual Disability / genetics
  • Intellectual Disability / pathology
  • MAP Kinase Kinase 5 / genetics
  • Neurons / cytology
  • Neurons / physiology
  • Obesity / genetics*
  • Polymorphism, Single Nucleotide
  • Protein Kinases / genetics
  • Quantitative Trait Loci
  • Sarcoplasmic Reticulum Calcium-Transporting ATPases / genetics
  • Transcription Factors / genetics
  • Transcriptome

Substances

  • Transcription Factors
  • Protein Kinases
  • SH3-binding domain kinase 1, human
  • MAP Kinase Kinase 5
  • MAP2K5 protein, human
  • Sarcoplasmic Reticulum Calcium-Transporting ATPases
  • ATP2A1 protein, human

Supplementary concepts

  • Simpson-Golabi-Behmel syndrome