Inducible CRISPRa screen identifies putative enhancers

J Genet Genomics. 2021 Oct 20;48(10):917-927. doi: 10.1016/j.jgg.2021.06.012. Epub 2021 Jul 15.

Abstract

Enhancers are critical cis-regulatory elements that regulate spatiotemporal gene expression and control cell fates. However, the identification of enhancers in native cellular contexts still remains a challenge. Here, we develop an inducible CRISPR activation (CRISPRa) system by transgenic expression of doxycycline (Dox)-inducible dCas9-VPR in mouse embryonic stem cells (iVPR ESC). With this line, a simple introduction of specific guide RNAs targeting promoters or enhancers allows us to realize the effect of CRISPRa in an inducible, reversible, and Dox concentration-dependent manner. Taking advantage of this system, we induce tiled CRISPRa across genomic regions (105 kilobases) surrounding T (Brachyury), one of the key mesodermal development regulator genes. Moreover, we identify several CRISPRa-responsive elements with chromatin features of putative enhancers, including a region the homologous sequence in which humans harbors a body height risk variant. Genetic deletion of this region in ESC does affect subsequent T gene activation and osteogenic differentiation. Therefore, our inducible CRISPRa ESC line provides a convenient platform for high-throughput screens of putative enhancers.

Keywords: CRISPR activation; Cis-regulatory elements; Enhancer; Screen.

MeSH terms

  • Animals
  • CRISPR-Cas Systems* / genetics
  • Cell Differentiation / genetics
  • Chromatin / genetics
  • Chromatin / metabolism
  • Clustered Regularly Interspaced Short Palindromic Repeats / genetics
  • Doxycycline / pharmacology
  • Enhancer Elements, Genetic* / genetics
  • Humans
  • Mice
  • Mouse Embryonic Stem Cells / cytology
  • Mouse Embryonic Stem Cells / metabolism

Substances

  • Doxycycline
  • Chromatin