Inherited Autoinflammatory Syndromes

Annu Rev Pathol. 2022 Jan 24:17:227-249. doi: 10.1146/annurev-pathmechdis-030121-041528. Epub 2021 Oct 26.

Abstract

Autoinflammation describes a collection of diverse diseases caused by indiscriminate activation of the immune system in an antigen-independent manner. The rapid advancement of genetic diagnostics has allowed for the identification of a wide array of monogenic causes of autoinflammation. While the clinical picture of these syndromes is diverse, it is possible to thematically group many of these diseases under broad categories that provide insight into the mechanisms of disease and therapeutic possibilities. This review covers archetypical examples of inherited autoinflammatory diseases in five major categories: inflammasomopathy, interferonopathy, unfolded protein/cellular stress response, relopathy, and uncategorized. This framework can suggest where future work is needed to identify other genetic causes of autoinflammation, what types of diagnostics need to be developed to care for this patient population, and which options might be considered for novel therapeutic targeting.

Keywords: genetics; immunology; inflammation.

Publication types

  • Review

MeSH terms

  • Autoimmune Diseases* / genetics
  • Autoimmune Diseases* / therapy
  • Hereditary Autoinflammatory Diseases* / diagnosis
  • Hereditary Autoinflammatory Diseases* / genetics
  • Hereditary Autoinflammatory Diseases* / therapy
  • Humans
  • Inflammation / genetics
  • Syndrome