Muir-Torre syndrome: a case of unusual coexisting genetic mutations

Clin Exp Dermatol. 2022 Mar;47(3):602-604. doi: 10.1111/ced.15008. Epub 2021 Dec 7.

Abstract

Patients with Muir-Torre syndrome (MTS) commonly have germline mismatch repair mutations in MLH1, MSH2 or MSH6, with a strong predominance in MSH2. A subset of approximately one-third of patients will instead have an autosomal recessive base excision repair mutation in MUTYH called MUTYH polyposis. To the best of our knowledge, this is the first report of coexisting germline MSH2 and MUTYH mutations in a patient with MTS.

Publication types

  • Case Reports
  • Letter

MeSH terms

  • Adult
  • DNA Glycosylases / genetics*
  • Diagnosis, Differential
  • Germ-Line Mutation*
  • Humans
  • Male
  • Muir-Torre Syndrome / diagnosis
  • Muir-Torre Syndrome / genetics*
  • Muir-Torre Syndrome / surgery
  • MutS Homolog 2 Protein / genetics*

Substances

  • DNA Glycosylases
  • mutY adenine glycosylase
  • MSH2 protein, human
  • MutS Homolog 2 Protein