Toxoplasmosis in patients with an autoimmune disease and immunosuppressive agents: A multicenter study and literature review

PLoS Negl Trop Dis. 2022 Aug 8;16(8):e0010691. doi: 10.1371/journal.pntd.0010691. eCollection 2022 Aug.

Abstract

Background: Cases of Toxoplasma reactivation or more severe primary infection have been reported in patients receiving immunosuppressive (IS) treatment for autoimmune diseases (AID). The purpose of this study was to describe features of toxoplasmosis occurring in patients with AID treated by IS therapy, excluded HIV-positive and transplant patients.

Methods: A multicenter descriptive study was conducted using data from the French National Reference Center for Toxoplasmosis (NRCT) that received DNA extracts or strains isolated from patients, associated with clinical data. Other cases were retrieved through a questionnaire sent to all French parasitology and internal medicine departments. Furthermore, a systematic literature review was conducted.

Results: 61 cases were collected: 25 retrieved by the NRCT and by a call for observations and 36 from a literature review. Half of the cases were attributed to reactivation (50.9%), and most of cases (49.2%) were cerebral toxoplasmosis. The most common associated AID were rheumatoid arthritis (28%) and most frequent treatments were antimetabolites (44.3%). Corticosteroids were involved in 60.7% of cases. Patients had a favorable outcome (50.8%) but nine did not survive. For 12 cases, a successful Toxoplasma strain characterization suggested the possible role of this parasitic factor in ocular cases.

Conclusion: Although this remains a rare condition, clinicians should be aware for the management of patients and for the choice of IS treatment.

Publication types

  • Systematic Review
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adrenal Cortex Hormones
  • Autoimmune Diseases* / complications
  • Autoimmune Diseases* / drug therapy
  • Humans
  • Immunosuppressive Agents / adverse effects
  • Multicenter Studies as Topic
  • Toxoplasma* / genetics
  • Toxoplasmosis, Cerebral*

Substances

  • Adrenal Cortex Hormones
  • Immunosuppressive Agents

Grants and funding

The French National Reference Center for Toxoplasmosis received financial support by Santé Publique France (the national public health agency, https://www.santepubliquefrance.fr) for genotyping study, but no author has personally received grant. The funder had no role in study design, data collection and analysis, decision to publish, or preparation of the manuscript.