Ileal bypass for pruritus relief in a 3-year-old boy with advanced progressive familial intrahepatic cholestasis: how effective is it?

Folia Med (Plovdiv). 2023 Feb 28;65(1):183-185. doi: 10.3897/folmed.65.e73628.

Abstract

Progressive familial intrahepatic cholestasis (PFIC) is a group of liver disorders that manifest in early childhood with cholestasis and pruritus resulting progressively in liver failure. We present a case of a 3-year-old boy with advanced PFIC from refractory pruritus. In order to offer an effective treatment of pruritus, our patient underwent ileal bypass and after a 2-month period free of symptoms, unexpectedly relapsed after a Rota viral infection. Finally, the child underwent orthotopic liver transplantation. Patients with advanced PFIC do not seem to benefit from nontransplant invasive interventions regarding the relief of pruritus.

Keywords: children; cholestasis; ileal bypass; pruritus.

Publication types

  • Case Reports

MeSH terms

  • Child
  • Child, Preschool
  • Cholestasis*
  • Cholestasis, Intrahepatic* / complications
  • Cholestasis, Intrahepatic* / genetics
  • Cholestasis, Intrahepatic* / surgery
  • Digestive System Surgical Procedures*
  • Diphenhydramine
  • Humans
  • Male
  • Pruritus / etiology

Substances

  • Diphenhydramine

Supplementary concepts

  • Cholestasis, progressive familial intrahepatic 1