Early Diagnosis of 46,XX Testicular Difference of Sexual Development: Unusual Presentation with Increased Nuchal Translucency

Fetal Pediatr Pathol. 2024 Mar-Apr;43(2):176-181. doi: 10.1080/15513815.2023.2274831. Epub 2023 Oct 30.

Abstract

Introduction: 46,XX testicular disorder of sexual development (DSD) may present prenatally as a mismatch between phenotype and karyotype. Enlarged nuchal translucency is an abnormal sign of many disorders. We present a first trimester fetus with increased nuchal translucency that was later determined to be a 46,XX testicular DSD.

Case presentation: A first-trimester pregnancy ultrasound revealed enlarged nuchal translucency. Chorionic villous sampling documented a 46,XX karyotype. Subsequent ultrasounds identified male external genitalia. FISH analysis documented a SRY gene translocation. At birth, the infant had normal male internal and external genitalia.

Conclusions: 46,XX testicular DSD may present in the first trimester with an enlarged nuchal translucency.

Keywords: 46,XX testicular DSD; enlarged nuchal translucency; hypergonadotropic hypogonadism; prenatal diagnosis.

Publication types

  • Case Reports

MeSH terms

  • Early Diagnosis
  • Female
  • Humans
  • Infant, Newborn
  • Karyotyping
  • Male
  • Nuchal Translucency Measurement*
  • Pregnancy
  • Pregnancy Trimester, First
  • Translocation, Genetic*