Clinicopathologic features of relapsed CD19(-) B-ALL in CD19-targeted immunotherapy: Biological insights into relapse and LILRB1 as a novel B-cell marker for CD19(-) B lymphoblasts

Int J Lab Hematol. 2024 Jun;46(3):503-509. doi: 10.1111/ijlh.14226. Epub 2024 Jan 4.

Abstract

Introduction: The mechanism of relapsed CD19(-) B-ALL after anti-CD19 immunotherapy (Kymriah [CART-19] and blinatumomab) is under active investigation. Our study aims to assess LILRB1 as a novel B-cell marker for detecting CD19(-) B-lymphoblasts and to analyze the clinicopathologic/genetic features of such disease to provide biological insight into relapse.

Methods: Six patients (3 males/3 females, median age of 14 years) with relapsed CD19(-) B-ALL were analyzed for cytogenetic/genetic profile and immunophenotype.

Results: CD19(-) B-ALL emerged after an interval of 5.8 months following anti-CD19 therapy. Five of six patients had B-cell aplasia, indicative of a persistent effect of CART or blinatumomab at relapse. Importantly, LILRB1 was variably expressed on CD19(-) and CD19(+) B lymphoblasts, strong on CD34(+) lymphoblasts and dim/partial on CD34(-) lymphoblasts. Three of six patients with paired B-ALL samples (pre- and post-anti-CD19 therapy) carried complex and different cytogenetic abnormalities, either as completely different or sharing a subset of cytogenetic abnormalities.

Conclusion: LILRB1 can be used as a novel B-cell marker to identify CD19(-) B lymphoblasts. The emergence of CD19(-) B-ALL appears to be associated with complex cytogenetic evolutions. The mechanism of CD19(-) B-ALL relapse under anti-CD19 immune pressure remains to be explored by comprehensive molecular studies.

Keywords: B‐ALL; CART‐19; LILRB1; blinatumomab; cytogenetics; immunotherapy; relapse.

MeSH terms

  • Adolescent
  • Adult
  • Antigens, CD / metabolism
  • Antigens, CD19*
  • B-Lymphocytes / immunology
  • B-Lymphocytes / metabolism
  • B-Lymphocytes / pathology
  • Biomarkers, Tumor
  • Child
  • Female
  • Humans
  • Immunophenotyping
  • Immunotherapy / methods
  • Leukocyte Immunoglobulin-like Receptor B1*
  • Male
  • Membrane Glycoproteins
  • Precursor B-Cell Lymphoblastic Leukemia-Lymphoma / diagnosis
  • Precursor B-Cell Lymphoblastic Leukemia-Lymphoma / immunology
  • Precursor B-Cell Lymphoblastic Leukemia-Lymphoma / metabolism
  • Precursor B-Cell Lymphoblastic Leukemia-Lymphoma / pathology
  • Precursor B-Cell Lymphoblastic Leukemia-Lymphoma / therapy
  • Receptors, Immunologic / genetics
  • Receptors, Immunologic / metabolism
  • Recurrence

Substances

  • Antigens, CD19
  • Leukocyte Immunoglobulin-like Receptor B1
  • LILRB1 protein, human
  • Receptors, Immunologic
  • Antigens, CD
  • CD19 molecule, human
  • Biomarkers, Tumor
  • Membrane Glycoproteins