Generation of an Alagille Syndrome (ALGS) patient-derived induced pluripotent stem cell line (TRNDi036-A) carrying a heterozygous mutation (p.Cys693*) in the JAG1 gene

Stem Cell Res. 2024 Jun:77:103429. doi: 10.1016/j.scr.2024.103429. Epub 2024 Apr 29.

Abstract

Alagille syndrome (ALGS) is an autosomal dominant, multisystemic disorder due to haploinsufficiency in JAG1 or less frequently, mutations in NOTCH2. The disease has been difficult to diagnose and treat due to variable expression. The generation of this iPSC line (TRNDi036-A) carrying a heterozygous mutation (p.Cys693*) in the JAG1 gene provides a means of studying the disease and developing novel therapeutics towards patient treatment.

MeSH terms

  • Alagille Syndrome* / genetics
  • Cell Line
  • Female
  • Heterozygote*
  • Humans
  • Induced Pluripotent Stem Cells* / metabolism
  • Jagged-1 Protein* / genetics
  • Jagged-1 Protein* / metabolism
  • Male
  • Mutation*

Substances

  • Jagged-1 Protein
  • JAG1 protein, human