TaqTth-hpRNA: a novel compact RNA-targeting tool for specific silencing of pathogenic mRNA

Genome Biol. 2024 Jul 7;25(1):179. doi: 10.1186/s13059-024-03326-3.

Abstract

Pathogenic allele silencing is a promising treatment for genetic hereditary diseases. Here, we develop an RNA-cleaving tool, TaqTth-hpRNA, consisting of a small, chimeric TaqTth, and a hairpin RNA guiding probe. With a minimal flanking sequence-motif requirement, in vitro and in vivo studies show TaqTth-hpRNA cleaves RNA efficiently and specifically. In an Alzheimer's disease model, we demonstrate silencing of mutant APPswe mRNA without altering the wild-type APP mRNA. Notably, due to the compact size of TaqTth, we are able to combine with APOE2 overexpression in a single AAV vector, which results in stronger inhibition of pathologies.

Keywords: AAV; APOE2; APP; Alzheimer’s disease; Hairpin RNA guiding probe; RNA cleaving; TaqTth.

MeSH terms

  • Alzheimer Disease* / genetics
  • Alzheimer Disease* / metabolism
  • Amyloid beta-Protein Precursor / genetics
  • Amyloid beta-Protein Precursor / metabolism
  • Animals
  • Dependovirus / genetics
  • Gene Silencing*
  • Genetic Vectors
  • Humans
  • Mice
  • RNA Cleavage
  • RNA, Messenger* / genetics
  • RNA, Messenger* / metabolism

Substances

  • RNA, Messenger
  • Amyloid beta-Protein Precursor