Pediatric therapy-related hematologic neoplasms show enrichment for KMT2A rearrangement and lymphoblastic phenotype

Leuk Lymphoma. 2024 Dec;65(12):1840-1852. doi: 10.1080/10428194.2024.2376166. Epub 2024 Aug 8.

Abstract

In children, therapy-related hematologic neoplasms (t-HN) are uncommon. Many are driven by genetic events independent of clonal hematopoiesis. We sought to understand the clinical and genetic factors of pediatric t-HN in a large independent cohort. Fifty-six t-HN were retrospectively identified. Chromosome microarray, next-generation and/or RNA sequencing were performed. Patients had primary hematologic, solid, or central nervous system tumors. t-HN included myeloid (t-MN) and lymphoblastic (t-ALL) phenotypes. Approximately half of the cases harbored KMTA2A rearrangement (KMT2Ar). Among t-HN without KMT2Ar, genetic drivers were heterogeneous, including diverse fusions or aneuploidy. Approximately 18% harbored 17p deletions and/or TP53 mutations. EFS/OS was not associated with t-HN lineage or KMT2Ar, but HSCT was associated with improved EFS and OS. We detail one of the largest cohorts to date of pediatric t-HN, confirming frequent KMT2Ar and t-ALL.

Keywords: KMT2A; Leukemia; pediatric; therapy-related.

MeSH terms

  • Adolescent
  • Child
  • Child, Preschool
  • Female
  • Gene Rearrangement*
  • Hematologic Neoplasms* / genetics
  • Hematologic Neoplasms* / therapy
  • Histone-Lysine N-Methyltransferase* / genetics
  • Humans
  • Infant
  • Male
  • Mutation
  • Myeloid-Lymphoid Leukemia Protein* / genetics
  • Neoplasms, Second Primary* / etiology
  • Neoplasms, Second Primary* / genetics
  • Phenotype*
  • Precursor Cell Lymphoblastic Leukemia-Lymphoma / diagnosis
  • Precursor Cell Lymphoblastic Leukemia-Lymphoma / genetics
  • Precursor Cell Lymphoblastic Leukemia-Lymphoma / pathology
  • Precursor Cell Lymphoblastic Leukemia-Lymphoma / therapy
  • Prognosis
  • Retrospective Studies

Substances

  • Histone-Lysine N-Methyltransferase
  • KMT2A protein, human
  • Myeloid-Lymphoid Leukemia Protein