Identification of SLC25A46 interaction interfaces with mitochondrial membrane fusogens Opa1 and Mfn2

J Biol Chem. 2024 Oct;300(10):107740. doi: 10.1016/j.jbc.2024.107740. Epub 2024 Aug 31.

Abstract

Mitochondrial fusion requires the sequential merger of four bilayers to two. The outer-membrane solute carrier family 25 member (SLC25A46) interacts with both the outer and inner membrane dynamin family GTPases mitofusin 1/2 and optic atrophy 1 (Opa1). While SLC25A46 levels are known to affect mitochondrial morphology, how SLC25A46 interacts with mitofusin 1/2 and Opa1 to regulate membrane fusion is not understood. In this study, we use crosslinking mass spectrometry and AlphaFold 2 modeling to identify interfaces mediating an SLC25A46 interaction with Opa1 and Mfn2. We reveal that the bundle signaling element of Opa1 interacts with SLC25A46, and present evidence of an Mfn2 interaction involving the SLC25A46 cytosolic face. We validate these newly identified interaction interfaces and show that they play a role in mitochondrial network maintenance.

Keywords: GTPase; mass spectrometry; membrane fusion; mitochondria; mitochondrial solute carrier; protein cross-linking; protein-protein interaction; structural model.

MeSH terms

  • GTP Phosphohydrolases* / chemistry
  • GTP Phosphohydrolases* / metabolism
  • Humans
  • Mitochondria / metabolism
  • Mitochondrial Dynamics
  • Mitochondrial Membrane Transport Proteins / chemistry
  • Mitochondrial Membrane Transport Proteins / genetics
  • Mitochondrial Membrane Transport Proteins / metabolism
  • Mitochondrial Membranes* / metabolism
  • Mitochondrial Proteins* / genetics
  • Mitochondrial Proteins* / metabolism
  • Phosphate Transport Proteins
  • Protein Binding

Substances

  • GTP Phosphohydrolases
  • OPA1 protein, human
  • MFN2 protein, human
  • Mitochondrial Proteins
  • SLC25A46 protein, human
  • Mitochondrial Membrane Transport Proteins
  • Phosphate Transport Proteins