Cerebral complications in Schimke immuno-osseous dysplasia

Eur J Pediatr. 1997 Oct;156(10):789-91. doi: 10.1007/s004310050714.

Abstract

Schimke immuno-osseous dysplasia is a multisystem disorder consisting of spondylo-epiphysial dysplasia, progressive renal insufficiency due to focal segmental glomerulosclerosis, and immunodeficiency. Cerebrovascular complications have only been described in five patients. Here we report a patient with prominent neurological symptoms most likely caused by transient ischaemic attacks.

Conclusion: Neurological symptoms consisted of repeated brief spells of hemiparaesthesia, motoric aphasia and diplopia. MRI studies of the CNS revealed progressive white matter lesions. Morphological changes as well as neurological deficits are compatible with cerebral ischaemia.

Publication types

  • Case Reports

MeSH terms

  • Brain / pathology
  • Child
  • Dwarfism / diagnosis*
  • Dwarfism / genetics
  • Dwarfism / immunology
  • Humans
  • Immunologic Deficiency Syndromes / diagnosis*
  • Immunologic Deficiency Syndromes / genetics
  • Immunologic Deficiency Syndromes / immunology
  • Ischemic Attack, Transient / diagnosis*
  • Ischemic Attack, Transient / genetics
  • Ischemic Attack, Transient / immunology
  • Magnetic Resonance Imaging
  • Male
  • Osteochondrodysplasias / diagnosis*
  • Osteochondrodysplasias / genetics
  • Osteochondrodysplasias / immunology
  • Syndrome