[Familial autoimmune hepatitis and C4 deficiency]

Rev Med Interne. 1998 Oct;19(10):731-3. doi: 10.1016/s0248-8663(98)80709-1.
[Article in French]

Abstract

Introduction: Familial auto-immune hepatitis is unusual. We report a case in which hepatitis was associated with a deficiency in the C4 component of the complement.

Exegesis: Type 1 auto-immune hepatitis A was diagnosed in a 38-year-old woman presenting with systemic lupus erythematosus. Her daughter had to undergo a splenectomy for immunologic thrombocytopenic purpura when she was 9 years old. When she turned 13, she further developed type 1 autoimmune hepatitis. During follow-up (4 and 8 years, respectively), both patients had a mild deficiency in C4.

Conclusion: C4 deficiency is not only frequently observed in relatives of patients with auto-immune hepatitis, but also in familial systemic lupus. This abnormality may have had a crucial pathogenic role in these two patients.

Publication types

  • Case Reports
  • English Abstract

MeSH terms

  • Adolescent
  • Adult
  • Complement C4 / deficiency*
  • Diagnosis, Differential
  • Female
  • Follow-Up Studies
  • Hepatitis A / complications
  • Hepatitis A / diagnosis
  • Hepatitis A / immunology*
  • Hepatitis, Autoimmune / complications
  • Hepatitis, Autoimmune / diagnosis
  • Hepatitis, Autoimmune / immunology*
  • Humans
  • Lupus Erythematosus, Systemic / complications
  • Lupus Erythematosus, Systemic / diagnosis
  • Lupus Erythematosus, Systemic / immunology
  • Purpura, Thrombocytopenic / complications
  • Purpura, Thrombocytopenic / diagnosis
  • Purpura, Thrombocytopenic / immunology
  • Time Factors

Substances

  • Complement C4