Clustering of distinct autoimmune diseases associated with functional abnormalities of T cell survival in children

Clin Exp Immunol. 2000 Jul;121(1):53-8. doi: 10.1046/j.1365-2249.2000.01275.x.

Abstract

To ascertain whether alterations of lymphocyte switching off may be associated with clustering of autoimmune diseases in children, Fas- and C2-ceramide-induced cell death was evaluated on T cell lines derived from three patients affected by clustering of autoimmune disorders. Three patterns were found: patient 3 was resistant to Fas- and C2-ceramide, patient 1 was resistant to Fas, but sensitive to C2-ceramide, patient 2 was resistant to C2-ceramide, but sensitive to Fas. By contrast, Fas- and C2-ceramide-induced cell death was normal in five children with systemic juvenile rheumatoid arthritis, five children with insulin-dependent diabetes and 10 age-matched healthy controls. Surface expression of Fas was low in patient 1, but normal in patients 2 and 3. Together with normal Fas transcripts, patients 2 and 3 displayed a transcript 152 bp longer than the normal one retaining intron 5. Our data indicate that polyreactive autoimmune syndromes may be associated with heterogeneous alteration of the immune response switching-off system.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adolescent
  • Apoptosis / drug effects
  • Apoptosis / immunology*
  • Autoimmune Diseases / blood
  • Autoimmune Diseases / genetics
  • Autoimmune Diseases / immunology*
  • Cell Survival
  • Cells, Cultured
  • Diabetes Mellitus, Type 1 / blood
  • Diabetes Mellitus, Type 1 / genetics
  • Diabetes Mellitus, Type 1 / immunology
  • Female
  • Humans
  • Immunophenotyping
  • Leukocytes, Mononuclear / classification
  • Leukocytes, Mononuclear / immunology
  • Male
  • Sphingosine / analogs & derivatives
  • Sphingosine / pharmacology
  • T-Lymphocytes / cytology*
  • T-Lymphocytes / drug effects
  • T-Lymphocytes / immunology*
  • fas Receptor / genetics
  • fas Receptor / metabolism

Substances

  • N-acetylsphingosine
  • fas Receptor
  • Sphingosine