The diabetes-prone BB rat carries a frameshift mutation in Ian4, a positional candidate of Iddm1

Diabetes. 2002 Jun;51(6):1972-9. doi: 10.2337/diabetes.51.6.1972.

Abstract

Diabetes-prone (DP) BB rats spontaneously develop insulin-dependent diabetes resembling human type 1 diabetes. They also exhibit lifelong T-cell lymphopenia. Functional and genetic data support the hypothesis that the gene responsible for the lymphopenia, Lyp, is also a diabetes susceptibility gene, named Iddm1. We constructed a 550-kb P1-derived artificial chromosome contig of the region. Here, we present a corrected genetic map reducing the genetic interval to 0.2 cM and the physical interval to 150-290 kb. A total of 13 genes and six GenomeScan models are assigned to the homologous human DNA segment on HSA7q36.1, 8 of which belong to the family of immune-associated nucleotides (Ian genes). Two of these are orthologous to mouse Ian1 and -4, both excellent candidates for Iddm1. In normal rats, they are expressed in the thymus and T-cell regions of the spleen. In the thymus of lymphopenic rats, Ian1 exhibits wild-type expression patterns, whereas Ian4 expression is reduced. Mutational screening of their coding sequences revealed a frameshift mutation in Ian4 among lymphopenic rats. The mutation results in a truncated protein in which the COOH-terminal 215 amino acids-including the anchor localizing the protein to the outer mitochondrial membrane-are replaced by 19 other amino acids. We propose that Ian4 is identical to Iddm1.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Amino Acid Sequence
  • Animals
  • Chromosome Mapping
  • Chromosomes, Human, Pair 7
  • Cloning, Molecular
  • DNA Mutational Analysis
  • Diabetes Mellitus, Type 1 / genetics*
  • Frameshift Mutation*
  • GTP-Binding Proteins / chemistry
  • GTP-Binding Proteins / genetics*
  • Gene Expression
  • Genetic Predisposition to Disease*
  • Humans
  • Membrane Proteins*
  • Molecular Sequence Data
  • Rats
  • Rats, Inbred BB
  • Reverse Transcriptase Polymerase Chain Reaction
  • Sequence Alignment

Substances

  • GIMAP4 protein, human
  • Ian4 protein, mouse
  • Membrane Proteins
  • GTP-Binding Proteins
  • Gimap4 protein, rat