T-cell large granular lymphocyte leukemia is characterized by massive TCRBV-restricted clonal CD8 expansion and a generalized overexpression of the effector cell marker CD57

Hematol J. 2003;4(1):18-25. doi: 10.1038/sj.thj.6200212.

Abstract

Introduction: Large granular lymphocyte leukemia (LGL) is a clonal lymphoproliferative disease of CD8+ T cells expressing the CD57 activation marker. It is, however, unknown whether the CD57+ population represents the LGL clone or not. We previously demonstrated that the clone can be found in both CD8+CD57+ and CD8+CD57- cells, indicating that the LGL clone also resides in the CD57- fraction.

Materials and methods: Here, we quantified the extent of the clonal CD8 expansion in LGL using T-cell receptor Vbeta (TCRBV)-specific monoclonal antibodies, and determined whether the CD4 population also contained skews. Furthermore, dominant TCRBV populations were assessed for clonal status using T-cell receptor-gamma (TCRG) PCR on genomic DNA.

Results: We show that the dominant TCRBV in LGL contains CD57+ and CD57- cells. Molecular analysis of CD8+CD57+ and CD8+CD57- subfractions of the dominant TCRBV by TCRG PCR demonstrates that indeed both fractions are clonal, and that the clone is absent from the dominant TCRBV-negative population. Furthermore, we show that CD57 overexpression is not restricted to the LGL clone, but a general phenomenon in CD8 cells of LGL patients.

Conclusion: We therefore conclude that the primary characteristic of LGL is a clonal expansion of CD8 cells, with a concomitant upregulation of CD57 on this clone and uninvolved cells.

MeSH terms

  • Adult
  • Aged
  • Autoimmune Diseases / immunology
  • Autoimmune Diseases / pathology
  • CD4-Positive T-Lymphocytes / chemistry
  • CD57 Antigens / analysis
  • CD8-Positive T-Lymphocytes / chemistry
  • CD8-Positive T-Lymphocytes / pathology*
  • Clone Cells / pathology
  • DNA, Neoplasm / analysis
  • Female
  • Flow Cytometry
  • Gene Rearrangement, beta-Chain T-Cell Antigen Receptor*
  • Humans
  • Leukemia, T-Cell / immunology
  • Leukemia, T-Cell / pathology*
  • Male
  • Middle Aged
  • Neoplastic Stem Cells / chemistry
  • Neoplastic Stem Cells / pathology*
  • Receptors, Antigen, T-Cell, alpha-beta / genetics*
  • T-Lymphocyte Subsets / chemistry

Substances

  • CD57 Antigens
  • DNA, Neoplasm
  • Receptors, Antigen, T-Cell, alpha-beta