P518/Qrfp sequence polymorphisms in SAMP6 osteopenic mouse

Genomics. 2007 Nov;90(5):629-35. doi: 10.1016/j.ygeno.2007.07.011. Epub 2007 Sep 17.

Abstract

Mice lacking GPR103A expression display osteopenia. Analysis of mouse quantitative trait loci literature associated with bone mineral density suggested GPR103A ligand P518/Qrfp (chromosome 2qB) as a candidate osteoporosis gene. Promoter and coding regions of mouse P518/Qrfp were sequenced from genomic DNA obtained from the osteoporosis-prone strain SAMP6 and control strains SAMR1, A/J, AKR/J, BALB/c, C3H/HeJ, C57BL/6J, and DBA/2J. Four single-nucleotide polymorphisms (SNPs) were identified in only SAMP6 genomic DNA, g.-1773 T-->C, g.110 A-->G (N37S), g.188 G-->A (R63K), and g.135 T-->C (H45H). The promoter SNP generated a novel neuron-restrictive silencing factor binding site, a repressor that decreases gene expression in nonneuronal tissues. TaqMan analysis demonstrated fivefold lower P518/Qrfp liver expression in SAMP6 versus SAMR1 or C57BL/6J control strains. Tissue distribution of human, mouse, and rat P518/Qrfp and its receptors showed expression in bone and spinal cord. A direct role for P518/Qrfp function in maintaining bone mineral density is suggested.

MeSH terms

  • Amino Acid Sequence
  • Animals
  • Bone Density
  • Bone Diseases, Metabolic / genetics*
  • Humans
  • Intercellular Signaling Peptides and Proteins
  • Ligands
  • Mice
  • Mice, Inbred Strains
  • Molecular Sequence Data
  • Open Reading Frames / genetics*
  • Peptides / genetics*
  • Polymorphism, Single Nucleotide / genetics*
  • Promoter Regions, Genetic / genetics*
  • Quantitative Trait, Heritable*
  • Rats
  • Receptors, G-Protein-Coupled / genetics*
  • Sequence Homology, Amino Acid
  • Tissue Distribution

Substances

  • Intercellular Signaling Peptides and Proteins
  • Ligands
  • Peptides
  • QRFP peptide
  • Qrfpr protein, mouse
  • Receptors, G-Protein-Coupled