A small molecule inhibitor of ubiquitin-specific protease-7 induces apoptosis in multiple myeloma cells and overcomes bortezomib resistance

Cancer Cell. 2012 Sep 11;22(3):345-58. doi: 10.1016/j.ccr.2012.08.007.

Abstract

Bortezomib therapy has proven successful for the treatment of relapsed/refractory, relapsed, and newly diagnosed multiple myeloma (MM); however, dose-limiting toxicities and the development of resistance limit its long-term utility. Here, we show that P5091 is an inhibitor of deubiquitylating enzyme USP7, which induces apoptosis in MM cells resistant to conventional and bortezomib therapies. Biochemical and genetic studies show that blockade of HDM2 and p21 abrogates P5091-induced cytotoxicity. In animal tumor model studies, P5091 is well tolerated, inhibits tumor growth, and prolongs survival. Combining P5091 with lenalidomide, HDAC inhibitor SAHA, or dexamethasone triggers synergistic anti-MM activity. Our preclinical study therefore supports clinical evaluation of USP7 inhibitor, alone or in combination, as a potential MM therapy.

Publication types

  • Research Support, N.I.H., Extramural

MeSH terms

  • Animals
  • Antineoplastic Agents / pharmacology*
  • Antineoplastic Agents / therapeutic use
  • Antineoplastic Combined Chemotherapy Protocols / pharmacology
  • Antineoplastic Combined Chemotherapy Protocols / therapeutic use
  • Apoptosis / drug effects*
  • Boronic Acids / pharmacology*
  • Boronic Acids / therapeutic use
  • Bortezomib
  • Cell Line, Tumor
  • Cyclin-Dependent Kinase Inhibitor p21 / antagonists & inhibitors
  • Dexamethasone / pharmacology
  • Dexamethasone / therapeutic use
  • Drug Resistance, Neoplasm / drug effects
  • Drug Therapy, Combination
  • Humans
  • Lenalidomide
  • Mice
  • Mice, SCID
  • Molecular Sequence Data
  • Multiple Myeloma / drug therapy*
  • Multiple Myeloma / enzymology
  • Multiple Myeloma / pathology
  • Neovascularization, Pathologic / drug therapy
  • Protease Inhibitors / pharmacology
  • Protease Inhibitors / therapeutic use
  • Proto-Oncogene Proteins c-mdm2 / metabolism
  • Pyrazines / pharmacology*
  • Pyrazines / therapeutic use
  • Random Allocation
  • Thalidomide / analogs & derivatives
  • Thalidomide / pharmacology
  • Thalidomide / therapeutic use
  • Thiophenes / pharmacology*
  • Thiophenes / therapeutic use
  • Ubiquitin Thiolesterase / antagonists & inhibitors*
  • Ubiquitin Thiolesterase / genetics
  • Ubiquitin-Specific Peptidase 7
  • Xenograft Model Antitumor Assays

Substances

  • Antineoplastic Agents
  • Boronic Acids
  • Cyclin-Dependent Kinase Inhibitor p21
  • P5091
  • Protease Inhibitors
  • Pyrazines
  • Thiophenes
  • Thalidomide
  • Bortezomib
  • Dexamethasone
  • MDM2 protein, human
  • Proto-Oncogene Proteins c-mdm2
  • USP7 protein, human
  • Ubiquitin Thiolesterase
  • Ubiquitin-Specific Peptidase 7
  • Lenalidomide