Thrombocytosis as a response to high interleukin-6 levels in cGMP-dependent protein kinase I mutant mice

Arterioscler Thromb Vasc Biol. 2013 Aug;33(8):1820-8. doi: 10.1161/ATVBAHA.113.301507. Epub 2013 Jun 20.

Abstract

Objective: The purpose of this study was to investigate the influence of cGMP-dependent kinase I (cGKI) on platelet production.

Approach and results: We used hematology analyser to measure platelet counts in conventional cGKI-null mutants (cGKI(L1/L1)), gene-targeted cGKIα/β rescue mice (referred to as cGKI-smooth muscle [SM]) in which cGKI expression is specifically restored only in SM, platelet factor 4-Cre(tg/+); cGKI(L2/L2) mice in which the cGKI protein was specifically deleted in the megakaryocyte/platelet lineage and cGKI-deficient bone marrow-chimeras. Thrombocytosis was detected in cGKI(L1/L1) and in cGKI-SM. In contrast, neither platelet factor 4-Cre(tg/+); cGKI(L2/L2) nor cGKI-deficient bone marrow-chimeras displayed a thrombocytosis phenotype, indicating that the high platelet count in cGKI(L1/L1) and cGKI-SM mutants is attributable to loss of an extrinsic signal rather than reflecting an intrinsic defect in megakaryopoiesis. Cytometric analyses further showed that stimulation of bone marrow-derived wild-type megakaryocytes in vitro using serum preparations obtained from cGKI-SM mutants strongly accelerated megakaryopoiesis, suggesting that the high platelet count develops in response to serum factors. Indeed, using ELISA assay, we found elevated levels of interleukin-6, a known stimulator of thrombopoiesis, in cGKI-SM mutant serum, whereas interleukin-6 levels were unaltered in platelet factor 4-Cre(tg/+); cGKI(L2/L2) mice and cGKI-deficient bone marrow-chimeras. Accordingly, antibody-mediated blockade of interleukin-6 normalized platelet counts in cGKI-SM mice.

Conclusions: Abnormal cGMP/cGKI signaling in nonhematopoietic cells affects thrombopoiesis via elevated interleukin-6 production and results in thrombocytosis in vivo. Dysfunction of cGMP/cGKI signaling in nonhematopoietic cells contributes to a high platelet count, which is potentially associated with thrombosis.

Keywords: cGMP-dependent protein kinase type I; interleukin-6; thrombopoiesis.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Animals
  • Blood Platelets / cytology
  • Blood Platelets / metabolism
  • Bone Marrow Cells / cytology
  • Bone Marrow Cells / metabolism
  • Cyclic GMP-Dependent Protein Kinase Type I / genetics*
  • Cyclic GMP-Dependent Protein Kinase Type I / metabolism*
  • Hematopoiesis / physiology
  • Hemostasis / physiology
  • Interleukin-6 / blood*
  • Megakaryocytes / cytology
  • Megakaryocytes / metabolism
  • Mice
  • Mice, Knockout
  • Phenotype
  • Platelet Count
  • Signal Transduction / physiology
  • Thrombocytosis / genetics*
  • Thrombocytosis / metabolism*

Substances

  • Interleukin-6
  • Cyclic GMP-Dependent Protein Kinase Type I