A case of Refsum disease with atypical clinical picture in family members

Ital J Neurol Sci. 1989 Aug;10(4):451-4. doi: 10.1007/BF02334952.

Abstract

A typical case of Refsum disease with high phytanic acid plasma levels is described. Two siblings showed some features but not the entire clinical spectrum of the disease. The unusual condition of the patient's father, a presumed heterozygotic carrier with characteristic bone abnormalities and a delayed onset retinopathy, is discussed.

Publication types

  • Case Reports

MeSH terms

  • Adult
  • Aged
  • Aged, 80 and over
  • Eicosanoic Acids / blood*
  • Female
  • Humans
  • Male
  • Middle Aged
  • Phytanic Acid / blood*
  • Refsum Disease / blood
  • Refsum Disease / genetics*
  • Refsum Disease / physiopathology

Substances

  • Eicosanoic Acids
  • Phytanic Acid