Phenotypical and molecular distinctness of sinonasal haemangiopericytoma compared to solitary fibrous tumour of the sinonasal tract

Histopathology. 2014 Nov;65(5):667-73. doi: 10.1111/his.12452. Epub 2014 Aug 4.

Abstract

Aims: Sinonasal haemangiopericytoma (SN-HPC) is a rare sinonasal mesenchymal neoplasm of perivascular myoid cell origin. Solitary fibrous tumour (SFT) occurs only very rarely in the sinonasal tract. SFT and soft tissue HPC have been considered a single entity. Recently, recurrent gene fusions involving NAB2-STAT6 resulting in differential expression of STAT6 were characterized as central molecular events in SFT. However, no data exist for NAB2-STAT6 status or STAT6 expression in SN-HPC.

Methods and results: We examined six SN-HPCs and two sinonasal SFTs by immunohistochemistry and RT-PCR for NAB2-STAT6 fusions. SN-HPC affected three females and three males (mean age: 72 years). They expressed smooth muscle actin, lacked strong CD34 reactivity and were negative for nuclear STAT6 expression. RT-PCR analysis confirmed the absence of NAB2-STAT6 fusions in all cases. Conversely, both sinonasal SFTs (in males aged 39 and 52 years) displayed classical features of pleuropulmonary and soft-tissue SFTs (uniformly CD34-positive with strong nuclear expression of STAT6). RT-PCR revealed NAB2-STAT6 fusions in both cases.

Conclusions: These findings confirm the molecular and phenotypical distinctness of these two entities. While SN-HPC is a site-specific sinonasal neoplasm of as yet unknown molecular pathogenesis, sinonasal SFTs show phenotypical and molecular identity to their pleural/extrapleural counterparts.

Keywords: NAB2; STAT6; gene fusion; head and neck; sinonasal haemangiopericytoma; solitary fibrous tumour.

MeSH terms

  • Adult
  • Aged
  • Aged, 80 and over
  • Biomarkers, Tumor / metabolism*
  • Female
  • Gene Fusion
  • Hemangiopericytoma / genetics
  • Hemangiopericytoma / metabolism
  • Hemangiopericytoma / pathology*
  • Humans
  • Immunohistochemistry
  • Male
  • Middle Aged
  • Nose Neoplasms / genetics
  • Nose Neoplasms / metabolism
  • Nose Neoplasms / pathology*
  • Organ Specificity
  • Phenotype
  • Repressor Proteins / genetics*
  • Repressor Proteins / metabolism
  • STAT6 Transcription Factor / genetics*
  • STAT6 Transcription Factor / metabolism
  • Solitary Fibrous Tumors / genetics
  • Solitary Fibrous Tumors / metabolism
  • Solitary Fibrous Tumors / pathology*

Substances

  • Biomarkers, Tumor
  • NAB2 protein, human
  • Repressor Proteins
  • STAT6 Transcription Factor
  • STAT6 protein, human