Combined chelation therapy with daily oral deferiprone and twice-weekly subcutaneous infusion of desferrioxamine in children with β-thalassemia: 3-year experience

Acta Haematol. 2015;133(2):226-36. doi: 10.1159/000363210. Epub 2014 Nov 11.

Abstract

Objective: To study the efficacy of combined treatment with oral and subcutaneous iron chelators.

Material and methods: 50-100 mg/kg/day of oral deferiprone (DFP) combined with 40 mg/kg/dose s.c. desferrioxamine (DFO) twice weekly were given to transfusion-dependent β-thalassemia children.

Results: Enrolled patients (9 with β-thalassemia major and 33 with β-thalassemia hemoglobin E), ranging from 3 to 18 years in age, were divided into 3 groups; group 1 ferritin ≥1,000-2,500 ng/ml (n = 10), group 2 ferritin >2,500-4,000 ng/ml (n = 23) and group 3 ferritin >4,000 ng/ml (n = 9). Of the 42 patients, 28 reached the 36-month follow-up. Ten patients whose ferritin declined <15% while receiving 100 mg/kg/day of DFP were considered nonresponders. The median age and previous transfusion duration before enrollment were significantly higher in nonresponders than responders (p = 0.04 and 0.003, respectively). The responders exhibited a significant fall in median ferritin levels from 2,954.6 to 936.6 ng/ml (p < 0.001). Time to a significant decrease in serum ferritin among responders was 6 months. In 13 patients, 16 episodes of adverse events occurred: hemophagocytosis with cytopenia (n = 1), neutropenia (n = 2), thrombocytopenia (n = 2), elevated alanine aminotransferase (n = 5), elevated serum creatinine (n = 1), proteinuria (n = 1) and gastrointestinal discomfort (n = 4).

Conclusion: Combination therapy with daily oral DFP and subcutaneous DFO twice weekly is a safe and effective alternative to chelation monotherapy in β-thalassemia children.

Publication types

  • Clinical Trial
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Administration, Oral
  • Adolescent
  • Alanine Transaminase / blood
  • Child
  • Child, Preschool
  • Creatinine / blood
  • Deferiprone
  • Deferoxamine / administration & dosage*
  • Deferoxamine / adverse effects
  • Drug Therapy, Combination / methods
  • Female
  • Ferritins / blood
  • Hemoglobin E / metabolism
  • Humans
  • Infusions, Subcutaneous
  • Male
  • Neutropenia / blood
  • Neutropenia / chemically induced
  • Pyridones / administration & dosage*
  • Pyridones / adverse effects
  • Siderophores / administration & dosage*
  • Siderophores / adverse effects
  • Thrombocytopenia / blood
  • Thrombocytopenia / chemically induced
  • beta-Thalassemia / blood
  • beta-Thalassemia / drug therapy*

Substances

  • Pyridones
  • Siderophores
  • Deferiprone
  • Ferritins
  • Hemoglobin E
  • Creatinine
  • Alanine Transaminase
  • Deferoxamine