Protein Quantitative Trait Loci Analysis Identifies Genetic Variation in the Innate Immune Regulator TOLLIP in Post-Lung Transplant Primary Graft Dysfunction Risk

Am J Transplant. 2016 Mar;16(3):833-40. doi: 10.1111/ajt.13525. Epub 2015 Dec 10.

Abstract

The authors previously identified plasma plasminogen activator inhibitor-1 (PAI-1) level as a quantitative lung injury biomarker in primary graft dysfunction (PGD). They hypothesized that plasma levels of PAI-1 used as a quantitative trait could facilitate discovery of genetic loci important in PGD pathogenesis. A two-stage cohort study was performed. In stage 1, they tested associations of loci with PAI-1 plasma level using linear modeling. Genotyping was performed using the Illumina CVD Bead Chip v2. Loci meeting a p < 5 × 10(-4) cutoff were carried forward and tested in stage 2 for association with PGD. Two hundred ninety-seven enrollees were evaluated in stage 1. Six loci, associated with PAI-1, were carried forward to stage 2 and evaluated in 728 patients. rs3168046 (Toll interacting protein [TOLLIP]) was significantly associated with PGD (p = 0.006). The increased risk of PGD for carrying at least one copy of this variant was 11.7% (95% confidence interval 4.9-18.5%). The false-positive rate for individuals with this genotype who did not have PGD was 6.1%. Variants in the TOLLIP gene are associated with higher circulating PAI-1 plasma levels and validate for association with clinical PGD. A protein quantitative trait analysis for PGD risk prioritizes genetic variations in TOLLIP and supports a role for Toll-like receptors in PGD pathogenesis.

Keywords: dysfunction; immune; inflammatory; ischemia reperfusion injury (IRI); lung (allograft) function; lung disease; lung transplantation; pulmonology; science; translational research.

Publication types

  • Multicenter Study
  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adult
  • Biomarkers / analysis*
  • Female
  • Follow-Up Studies
  • Genetic Variation / genetics*
  • Genotype
  • Humans
  • Intracellular Signaling Peptides and Proteins / genetics*
  • Lung Transplantation / adverse effects*
  • Male
  • Middle Aged
  • Phenotype
  • Plasminogen Activator Inhibitor 1 / blood
  • Primary Graft Dysfunction / blood
  • Primary Graft Dysfunction / diagnosis*
  • Primary Graft Dysfunction / etiology
  • Prognosis
  • Prospective Studies
  • Quantitative Trait Loci*

Substances

  • Biomarkers
  • Intracellular Signaling Peptides and Proteins
  • Plasminogen Activator Inhibitor 1
  • SERPINE1 protein, human
  • TOLLIP protein, human