Effect of anti-sclerostin therapy and osteogenesis imperfecta on tissue-level properties in growing and adult mice while controlling for tissue age

Bone. 2016 Mar:84:222-229. doi: 10.1016/j.bone.2016.01.001. Epub 2016 Jan 6.

Abstract

Bone composition and biomechanics at the tissue-level are important contributors to whole bone strength. Sclerostin antibody (Scl-Ab) is a candidate anabolic therapy for the treatment of osteoporosis that increases bone formation, bone mass, and bone strength in animal studies, but its effect on bone quality at the tissue-level has received little attention. Pre-clinical studies of Scl-Ab have recently expanded to include diseases with altered collagen and material properties such as osteogenesis imperfecta (OI). The purpose of this study was to investigate the role of Scl-Ab on bone quality by determining bone material composition and tissue-level mechanical properties in normal wild type (WT) tissue, as well as mice with a typical OI Gly➔Cys mutation (Brtl/+) in type I collagen. Rapidly growing (3-week-old) and adult (6-month-old) WT and Brtl/+ mice were treated for 5weeks with Scl-Ab. Fluorescent guided tissue-level bone composition analysis (Raman spectroscopy) and biomechanical testing (nanoindentation) were performed at multiple tissue ages. Scl-Ab increased mineral to matrix in adult WT and Brtl/+ at tissue ages of 2-4wks. However, no treatment related changes were observed in mineral to matrix levels at mid-cortex, and elastic modulus was not altered by Scl-Ab at any tissue age. Increased mineral-to-matrix was phenotypically observed in adult Brtl/+ OI mice (at tissue ages>3wks) and rapidly growing Brtl/+ (at tissue ages>4wks) mice compared to WT. At identical tissue ages defined by fluorescent labels, adult mice had generally lower mineral to matrix ratios and a greater elastic modulus than rapidly growing mice, demonstrating that bone matrix quality can be influenced by animal age and tissue age alike. In summary, these data suggest that Scl-Ab alters the matrix chemistry of newly formed bone while not affecting the elastic modulus, induces similar changes between Brtl/+ and WT mice, and provides new insight into the interaction between tissue age and animal age on bone quality.

Keywords: Anabolic therapy; Bone quality; Nanoindentation; Osteogenesis imperfecta; Raman spectroscopy; Sclerostin antibody.

Publication types

  • Research Support, N.I.H., Extramural

MeSH terms

  • Adaptor Proteins, Signal Transducing
  • Aging / pathology*
  • Animals
  • Antibodies / pharmacology
  • Antibodies / therapeutic use*
  • Bone Matrix / drug effects
  • Bone Matrix / metabolism
  • Bone and Bones / drug effects
  • Bone and Bones / metabolism
  • Bone and Bones / pathology*
  • Elastic Modulus / drug effects
  • Female
  • Femur / drug effects
  • Femur / metabolism
  • Femur / pathology
  • Genotype
  • Glycoproteins / immunology*
  • Intercellular Signaling Peptides and Proteins
  • Mice, Inbred C57BL
  • Minerals / metabolism
  • Osteogenesis Imperfecta / drug therapy*
  • Osteogenesis Imperfecta / pathology*

Substances

  • Adaptor Proteins, Signal Transducing
  • Antibodies
  • Glycoproteins
  • Intercellular Signaling Peptides and Proteins
  • Minerals
  • Sost protein, mouse