RNA splicing is a primary link between genetic variation and disease

Science. 2016 Apr 29;352(6285):600-4. doi: 10.1126/science.aad9417. Epub 2016 Apr 28.

Abstract

Noncoding variants play a central role in the genetics of complex traits, but we still lack a full understanding of the molecular pathways through which they act. We quantified the contribution of cis-acting genetic effects at all major stages of gene regulation from chromatin to proteins, in Yoruba lymphoblastoid cell lines (LCLs). About ~65% of expression quantitative trait loci (eQTLs) have primary effects on chromatin, whereas the remaining eQTLs are enriched in transcribed regions. Using a novel method, we also detected 2893 splicing QTLs, most of which have little or no effect on gene-level expression. These splicing QTLs are major contributors to complex traits, roughly on a par with variants that affect gene expression levels. Our study provides a comprehensive view of the mechanisms linking genetic variation to variation in human gene regulation.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Cell Line
  • Chromatin / metabolism
  • Gene Expression Regulation*
  • Genetic Variation*
  • Genome-Wide Association Study
  • Humans
  • Immune System Diseases / genetics*
  • Lymphocytes / immunology
  • Phenotype
  • Polymorphism, Single Nucleotide
  • Quantitative Trait Loci*
  • RNA Splicing / genetics*

Substances

  • Chromatin